TTC8 (BBS8) — Gene Review Notes

UniProt: Q8TAM2 | HGNC:20087 | Gene: TTC8 (synonym BBS8) | 541 aa | Chr 14

Summary of function

TTC8/BBS8 is a tetratricopeptide-repeat (TPR) superhelical protein and one of the eight
core subunits of the BBSome (BBS1, BBS2, BBS4, BBS5, BBS7, BBS8/TTC8, BBS9, BBIP10/BBIP1).
The BBSome is a coat-like, octameric adaptor that traffics specific membrane/signaling
proteins (GPCRs and other cargo) into and out of the primary cilium, coupled to intraflagellar
transport (IFT) and the small GTPase ARL6/BBS3. It also cooperates with the Rab8 GEF
Rabin8/RAB3IP to promote ciliary membrane biogenesis. Loss of function causes Bardet–Biedl
syndrome type 8 (BBS8, MIM:615985) and nonsyndromic retinitis pigmentosa 51 (RP51, MIM:613464).

Key evidence

Isoforms

Five isoforms (Q8TAM2-1..-6). A retina-specific exon is important in photoreceptors; a splice-site
mutation in a retina-specific exon causes nonsyndromic RP51 [UniProt; PMID:20451172]. GOA
annotations are not isoform-tagged, so no isoform field is added per-annotation.

Curation reasoning highlights