LRFN5

UniProt ID: Q96NI6
Organism: Homo sapiens
Review Status: COMPLETE
📝 Provide Detailed Feedback

Gene Description

LRFN5 (SALM5) is a neuronal type-I single-pass cell-surface adhesion protein with extracellular leucine-rich-repeat, immunoglobulin-like, and fibronectin type III domains. At synapses, its LRR-Ig ectodomain binds LAR-family receptor protein tyrosine phosphatases; isolated ectodomain fragments form 2:2 SALM5-PTPδ assemblies, and SALM5 dimerization supports induction of excitatory and inhibitory presynaptic differentiation. LRFN5 lacks the C-terminal PDZ-binding motif present in SALM1-SALM3 and therefore is not a canonical PDZ-tail recruiter of PSD-95. Its LRR region also binds HVEM/TNFRSF14 and contributes to suppression of macrophage activation and inflammatory responses in the central nervous system.

Existing Annotations Review

GO Term Evidence Action Reason
GO:0098839 postsynaptic density membrane
IBA
GO_REF:0000033
ACCEPT
Summary: The phylogenetic inference places LRFN5/SALM5 at the postsynaptic density membrane using a SALM5 family node and the exact rat Lrfn5 ortholog.
Reason: RGD:1309357 is rat Lrfn5/SALM5, whose annotation record carries direct SALM5-specific postsynaptic-density evidence. The LRFN5-specific PANTHER node and conserved type-I synaptic membrane architecture support this core transfer without importing PDZ-scaffold interactions from SALM1-SALM3; SALM5 lacks a cytoplasmic PDZ-binding motif.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
PANTHER:PTN000690490 · LRFN5/SALM5 phylogenetic node SUPPORTS TRANSFER
RGD:1309357 · rat Lrfn5/SALM5 SUPPORTS TRANSFER
GO:0009986 cell surface
IBA
GO_REF:0000033
ACCEPT
Summary: The IBA assigns cell-surface localization from the exact mouse Lrfn5 ortholog and an LRFN5/SALM5 phylogenetic node.
Reason: LRFN5 is a signal-peptide-bearing, single-pass type-I membrane protein, and MGI:MGI:2144814 is mouse Lrfn5/SALM5 with direct cell-surface evidence. This is a secure core localization transfer.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
MGI:MGI:2144814 · mouse Lrfn5/SALM5 SUPPORTS TRANSFER
PANTHER:PTN000690490 · LRFN5/SALM5 phylogenetic node SUPPORTS TRANSFER
GO:0098978 glutamatergic synapse
IBA
GO_REF:0000033
ACCEPT
Summary: The IBA places LRFN5/SALM5 at glutamatergic synapses using the exact mouse ortholog and an LRFN5-specific phylogenetic node.
Reason: The mouse Lrfn5 donor has gene-specific experimental evidence for localization at excitatory synapses. The transfer is consistent with SALM5's postsynaptic adhesion role and does not imply the glutamate-receptor-binding activities reported for SALM1 or SALM2.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
MGI:MGI:2144814 · mouse Lrfn5/SALM5 SUPPORTS TRANSFER
PANTHER:PTN000690490 · LRFN5/SALM5 phylogenetic node SUPPORTS TRANSFER
GO:0098982 GABA-ergic synapse
IBA
GO_REF:0000033
ACCEPT
Summary: The IBA places LRFN5/SALM5 at GABA-ergic synapses using the exact mouse ortholog and an LRFN5-specific phylogenetic node.
Reason: Mouse Lrfn5 has direct SALM5-specific evidence at inhibitory synapses, so the orthology transfer is sound. This localization is distinct from the paralog-specific postsynaptic receptor-organizing roles of SALM1 and SALM2.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
MGI:MGI:2144814 · mouse Lrfn5/SALM5 SUPPORTS TRANSFER
PANTHER:PTN000690490 · LRFN5/SALM5 phylogenetic node SUPPORTS TRANSFER
GO:0099560 synaptic membrane adhesion
IBA
GO_REF:0000033
ACCEPT
Summary: The IBA assigns synaptic membrane adhesion from a SALM5-specific phylogenetic node and the exact rat Lrfn5 ortholog.
Reason: Rat SALM5 has gene-specific experimental support for transsynaptic adhesion, and human SALM5 binds all three presynaptic LAR-family receptor phosphatases. The inference reflects a core SALM5 role rather than the SALM3/LRFN4 or SALM1/SALM2 mechanisms.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
PANTHER:PTN000690490 · LRFN5/SALM5 phylogenetic node SUPPORTS TRANSFER
RGD:1309357 · rat Lrfn5/SALM5 SUPPORTS TRANSFER
GO:1905606 regulation of presynapse assembly
IBA
GO_REF:0000033
MODIFY
Summary: SALM5 induces presynaptic differentiation in contacting axons, so the phylogenetic assignment is correct but lacks the experimentally supported positive direction.
Reason: The exact mouse Lrfn5 donor has direct SALM5-specific presynapse- induction evidence. GO:1905608 captures positive regulation of presynapse assembly more precisely than the unsigned parent term and avoids conflating SALM5 with SALM4/LRFN3-mediated inhibition of presynapse assembly.
Propagation Review
Root cause: TERM SCOPING PROBLEM
Failure modes: GRANULARITY MISMATCH
Sources checked:
MGI:MGI:2144814 · mouse Lrfn5/SALM5 SUPPORTS TRANSFER
The donor experiments show induction rather than inhibition of presynaptic differentiation.
PANTHER:PTN000690490 · LRFN5/SALM5 phylogenetic node SUPPORTS TRANSFER
GO:0016020 membrane
IEA
GO_REF:0000044
ACCEPT
Summary: UniProt subcellular-location vocabulary mapping assigns the broad membrane term to LRFN5.
Reason: Human LRFN5 has a cleaved signal peptide and a single transmembrane helix, while more specific cell-surface and synaptic membrane locations are independently supported. The broad membrane location is correct.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
UniProtKB-SubCell:SL-0162 · membrane controlled vocabulary SUPPORTS TRANSFER
GO:0005515 protein binding
IPI
PMID:32822567
A Human IgSF Cell-Surface Interactome Reveals a Complex Netw...
MODIFY
Summary: The human cell-surface interactome study supports LRFN5/SALM5 binding to PTPRF, PTPRD, and PTPRS, but generic protein binding obscures the cell-adhesion-molecule context.
Reason: The exact ordered WITH/FROM set encodes the three LAR-family receptor phosphatases. Their extracellular binding to human SALM5 is directly tested and is central to transsynaptic adhesion; GO:0050839 is more informative than GO:0005515 without asserting an unsupported catalytic or receptor activity.
Proposed replacements: cell adhesion molecule binding
Supporting Evidence:
PMID:32822567
With the exception of PTPRF-SALM4, we observed binding of all LAR-PTPRs to all SALMs
GO:0009986 cell surface
IEA
GO_REF:0000107
ACCEPT
Summary: Ensembl Compara transfers cell-surface localization from mouse Lrfn5/SALM5 to human LRFN5.
Reason: Q8BXA0 and ENSMUSP00000113123 represent the exact mouse Lrfn5 ortholog, whose record carries direct cell-surface evidence. Conserved signal-peptide and type-I membrane topology independently support transfer.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
UniProtKB:Q8BXA0 · mouse Lrfn5/SALM5 SUPPORTS TRANSFER
ensembl:ENSMUSP00000113123 · mouse Lrfn5 protein SUPPORTS TRANSFER
GO:0043031 negative regulation of macrophage activation
IEA
GO_REF:0000107
ACCEPT
Summary: Ensembl Compara transfers SALM5-dependent suppression of macrophage activation from the exact mouse Lrfn5 ortholog.
Reason: The donor is mouse Lrfn5/SALM5, not SALM3/LRFN4, and its annotation derives from direct CNS inflammation and macrophage-activation experiments. Human SALM5-HVEM binding is independently demonstrated in the same study, supporting conservation of this distinctive LRFN5 immune-regulatory role.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
UniProtKB:Q8BXA0 · mouse Lrfn5/SALM5 SUPPORTS TRANSFER
ensembl:ENSMUSP00000113123 · mouse Lrfn5 protein SUPPORTS TRANSFER
GO:0098839 postsynaptic density membrane
IEA
GO_REF:0000107
ACCEPT
Summary: Ensembl transfers postsynaptic-density-membrane localization from the exact rat Lrfn5/SALM5 ortholog.
Reason: D4A1J9 and ENSRNOP00000007600 are rat Lrfn5, whose record has direct SALM5-specific postsynaptic-density evidence. This is a secure exact- ortholog transfer and does not depend on the PDZ-binding tails of SALM1-SALM3.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
UniProtKB:D4A1J9 · rat Lrfn5/SALM5 SUPPORTS TRANSFER
ensembl:ENSRNOP00000007600 · rat Lrfn5 protein SUPPORTS TRANSFER
GO:0098978 glutamatergic synapse
IEA
GO_REF:0000107
ACCEPT
Summary: Ensembl transfers glutamatergic-synapse localization from mouse Lrfn5/SALM5.
Reason: The source is the exact mouse ortholog with gene-specific SALM5 experimental support at excitatory synapses. The localization does not imply the glutamate-receptor-binding functions reported for other SALM paralogs.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
UniProtKB:Q8BXA0 · mouse Lrfn5/SALM5 SUPPORTS TRANSFER
ensembl:ENSMUSP00000113123 · mouse Lrfn5 protein SUPPORTS TRANSFER
GO:0098982 GABA-ergic synapse
IEA
GO_REF:0000107
ACCEPT
Summary: Ensembl transfers GABA-ergic-synapse localization from mouse Lrfn5/SALM5.
Reason: Mouse Lrfn5 is the exact ortholog and has SALM5-specific evidence at inhibitory synapses. This is a gene-specific transfer rather than a generic SALM-family extrapolation.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
UniProtKB:Q8BXA0 · mouse Lrfn5/SALM5 SUPPORTS TRANSFER
ensembl:ENSMUSP00000113123 · mouse Lrfn5 protein SUPPORTS TRANSFER
GO:0099560 synaptic membrane adhesion
IEA
GO_REF:0000107
ACCEPT
Summary: Ensembl transfers synaptic membrane adhesion from rat Lrfn5/SALM5 to the human ortholog.
Reason: The donor is the exact rat ortholog with direct gene-specific support for SALM5 transsynaptic adhesion. Human SALM5 binding to LAR-family receptor phosphatases further supports this core role.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
UniProtKB:D4A1J9 · rat Lrfn5/SALM5 SUPPORTS TRANSFER
ensembl:ENSRNOP00000007600 · rat Lrfn5 protein SUPPORTS TRANSFER
GO:1905606 regulation of presynapse assembly
IEA
GO_REF:0000107
MODIFY
Summary: SALM5 induces presynaptic differentiation, so the exact-ortholog transfer is correct but should record the positive regulatory direction.
Reason: Q8BXA0 is mouse Lrfn5/SALM5, and its donor annotation traces to direct SALM5 induction experiments. GO:1905608 captures the positive effect while distinguishing LRFN5 from the inhibitory SALM4/LRFN3 cis mechanism.
Propagation Review
Root cause: TERM SCOPING PROBLEM
Failure modes: GRANULARITY MISMATCH
Sources checked:
UniProtKB:Q8BXA0 · mouse Lrfn5/SALM5 SUPPORTS TRANSFER
The gene-specific donor evidence shows induction of presynaptic differentiation.
ensembl:ENSMUSP00000113123 · mouse Lrfn5 protein SUPPORTS TRANSFER
GO:0005515 protein binding
IPI
PMID:27152329
Neuron-specific SALM5 limits inflammation in the CNS via its...
MODIFY
Summary: Human SALM5 directly binds the tumor-necrosis-factor-receptor-family member HVEM/TNFRSF14, but generic protein binding hides the partner class.
Reason: Q92956 is human HVEM/TNFRSF14. The study directly screened human SALM5 and human HVEM and mapped the conserved interaction; GO:0032813 precisely captures binding to a tumor necrosis factor receptor superfamily member without assigning SALM5 an intrinsic receptor-signaling activity.
Supporting Evidence:
PMID:27152329
Using hHVEM-Ig fusion protein to screen the library, we further validated the specificity of this interaction between SALM5 and HVEM.
GO:0043031 negative regulation of macrophage activation
ISS
GO_REF:0000024
ACCEPT
Summary: Curator-reviewed sequence-similarity transfer assigns suppression of macrophage activation from mouse Lrfn5/SALM5 to human LRFN5.
Reason: Q8BXA0 is the exact mouse Lrfn5 ortholog and has direct experimental support for SALM5-mediated macrophage suppression in CNS inflammatory models. The same study directly validates human SALM5-HVEM binding, supporting the conservation judgment while keeping the mouse in-vivo context explicit.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
UniProtKB:Q8BXA0 · mouse Lrfn5/SALM5 SUPPORTS TRANSFER
GO:0050728 negative regulation of inflammatory response
IDA
PMID:27152329
Neuron-specific SALM5 limits inflammation in the CNS via its...
ACCEPT
Summary: SALM5 suppresses inflammatory responses in the central nervous system through its interaction with HVEM; the live occurs_in CNS extension is retained.
Reason: The paper directly tests human SALM5-HVEM binding and shows SALM5- dependent suppression of inflammation in mouse CNS models. Although the in-vivo inflammatory phenotype is mouse, this is an experimental curator annotation to human LRFN5 from a full-text study that explicitly includes the human proteins; curator deference is appropriate.
Supporting Evidence:
PMID:27152329
We found that SALM5 suppressed lipopolysaccharide-induced inflammatory responses in the CNS and that a SALM-specific monoclonal antibody promoted inflammation in the CNS, and thereby aggravated clinical symptoms of mouse experimental autoimmune encephalomyelitis.
GO:0098632 cell-cell adhesion mediator activity
ISO
PMID:18227064
The SALM family of adhesion-like molecules forms heteromeric...
NEW
Summary: Rat Lrfn5/SALM5 mediates homophilic trans-cellular adhesion in heterologous-cell assays, supporting transfer of cell-cell adhesion mediator activity to human LRFN5.
Reason: GO:0098632 captures the demonstrated adhesion-mediating activity more precisely than generic binding. The evidence establishes homophilic SALM5-SALM5 adhesion across apposed cells, whereas the distinct SALM5-LAR-RPTP interaction supports heterophilic synaptic organization. D4A1J9 is the exact rat Lrfn5 ortholog, so the species boundary remains explicit.
Propagation Review
Root cause: NO FAILURE CORE
Sources checked:
UniProtKB:D4A1J9 · rat Lrfn5/SALM5 SUPPORTS TRANSFER
Supporting Evidence:
PMID:18227064
Both SALMs 4 and 5 formed homophilic, but not heterophilic associations, whereas no trans associations were formed by the other SALMs.
PMID:27225731
We found that SALM5-expressing cells coaggregated with cells expressing all three LAR-RPTPs (LAR, PTPδ, and PTPσ).

Core Functions

At the postsynaptic cell surface, the LRFN5 LRR-Ig ectodomain binds the cell-adhesion receptors PTPRF, PTPRD, and PTPRS. Structures of isolated human SALM5 and PTPδ ectodomain fragments show a 2:2 assembly in which an SALM5 dimer bridges two PTPδ molecules, and dimer-disrupting substitutions impair presynapse-inducing activity. Together with full-length rodent SALM5 perturbation, this supports a transsynaptic organizer activity that promotes excitatory and inhibitory presynaptic differentiation and synaptic membrane adhesion. The preferred LAR-RPTP mini-exon-B state remains unresolved.

Supporting Evidence:
  • PMID:27225731
    We found that SALM5-expressing cells coaggregated with cells expressing all three LAR-RPTPs (LAR, PTPδ, and PTPσ).
  • PMID:32822567
    With the exception of PTPRF-SALM4, we observed binding of all LAR-PTPRs to all SALMs
  • PMID:29348579
    For the SALM5/PTPδ complex crystal, the asymmetric unit contained one dimeric complex, in a 2:2 stoichiometry, where a central SALM5 dimer bridges two monomeric PTPδ molecules together.
  • PMID:29348579
    This meant that R110N/E160S mutation abrogated the capacity of SALM5 to induce presynaptic differentiation. Taken together, disrupting SALM5 dimerization may significantly impair its functionality in mediating presynaptic differentiation.
  • PMID:20410109
    We found that expression of the SALM family proteins SALM3 and SALM5 in nonneural and neural cells induces both excitatory and inhibitory presynaptic differentiation in contacting axons.

At the neuronal cell surface, the LRFN5 LRR region binds the tumor-necrosis- factor-receptor-family member HVEM/TNFRSF14. Direct human-protein experiments establish the selective binding activity, while mouse cell and disease-model experiments link SALM5-HVEM engagement to suppression of macrophage activation and inflammatory responses in the central nervous system. The immune phenotypes have not been demonstrated directly in human neural tissue.

Supporting Evidence:
  • PMID:27152329
    Using hHVEM-Ig fusion protein to screen the library, we further validated the specificity of this interaction between SALM5 and HVEM.
  • PMID:27152329
    The LRR domain, but not the Ig or FN domain from SALM5, is sufficient to endow the binding capacity to HVEM
  • PMID:27152329
    As shown in Fig. 2C, the production of both IL-6 and TNFα from the cultured macrophages was significantly inhibited by SALM5+ HEK293T cells. Therefore, SALM5 directly suppressed macrophage activation, likely by engaging a putative receptor on macrophages.

References

Loading supporting content…

Download this section (compressed HTML)

Suggested Questions for Experts

Q: Which mini-exon combinations of PTPRF, PTPRD, and PTPRS engage endogenous LRFN5 in human neurons, and why do membrane aggregation and purified-protein assays report opposite effects of mini-exon B?

Q: Does endogenous full-length human LRFN5 form a defined 2:2 transsynaptic assembly, and which LAR-RPTP partners dominate at excitatory versus inhibitory synapses?

Q: How much of LRFN5-dependent presynaptic differentiation requires heterophilic LAR-RPTP binding versus homophilic SALM5-SALM5 adhesion?

Q: Does human neuronal LRFN5-HVEM engagement suppress microglial or macrophage activation in the CNS, and which cell-autonomous signaling steps mediate the effect?

Suggested Experiments

Experiment: Create isogenic human induced-pluripotent-stem-cell-derived neurons with LRFN5 knockout, structure-guided LAR-binding substitutions, or dimer-disrupting substitutions and repair each allele at the endogenous locus. In paired pre/postsynaptic cultures, quantify surface delivery, transsynaptic proximity, synapsin and active-zone assembly, excitatory and inhibitory synapse numbers, and miniature synaptic currents.

Hypothesis: Endogenous human LRFN5 promotes presynapse assembly through an extracellular dimerization-dependent interaction with a partner-selective subset of LAR-RPTPs.

Type: Endogenous human-neuron structure-function analysis

Experiment: Express matched human PTPRF, PTPRD, and PTPRS mini-exon variants at comparable abundance, then measure SALM5 binding by SPR, cell-surface aggregation, and direction-resolved human-neuron coculture. Couple binding measurements to presynaptic differentiation and rescue with interface-specific mutants.

Hypothesis: LAR-RPTP mini-exon B has a context-dependent effect on LRFN5 binding that differs between soluble ectodomains and membrane-confined synaptic contacts.

Type: LAR-RPTP splice-code reconciliation

Experiment: Build human neuron-microglia and neuron-macrophage cocultures with cell-type- specific CRISPR disruption of LRFN5 or TNFRSF14. Restore wild-type or binding-defective proteins and measure contact-dependent cytokine responses, NF-κB pathway activation, cell-state transitions, and neuronal synaptic integrity.

Hypothesis: Human neuronal LRFN5 suppresses innate immune activation through direct engagement of HVEM on macrophages or microglia.

Type: Human CNS neuroimmune interface dissection

Knowledge Gaps

What is not known — curated, literature-grounded statements of the open unknowns (the inverse of core functions).

Gap: Which LAR-RPTP splice forms bind endogenous full-length LRFN5 at synapses is unresolved, especially because cell-aggregation assays and purified-protein measurements report opposite effects of mini-exon B.

OPEN BIOLOGY RESIDUAL_SUBGAP

What is known: A 2016 cell-aggregation study found that mini-exon B strongly inhibits SALM5-LAR-RPTP interactions, whereas two 2018 structural and SPR studies found that mini-exon B favors PTPδ binding. These assay systems differ in constructs, membrane context, and species and do not establish the occupied splice form in vivo.

Significance: The splice code may determine when and where the SALM5 organizer is engaged and is necessary for interpreting partner-selective synaptic phenotypes.

What would resolve it: Compare matched human PTPRF, PTPRD, and PTPRS mini-exon variants using purified kinetics, membrane-tethered binding, and endogenous pre-to-postsynaptic contacts in paired human neurons.

Provenance (the field's own admissions):

Gap: The stoichiometry, membrane directionality, and partner hierarchy of endogenous full-length human LRFN5 complexes at excitatory and inhibitory synapses are not established.

OPEN BIOLOGY RESIDUAL_SUBGAP

What is known: Human ectodomain fragments bind all three LAR-RPTPs, isolated LRR-Ig fragments form 2:2 assemblies with PTPδ, and rodent full-length SALM5 promotes presynaptic differentiation. Fragment structures and heterologous assays do not establish an obligate stable 2:2 complex or partner occupancy in human neurons.

Significance: Resolving the native assembly is required to connect the structural recognition mechanism to physiological synaptic organization without overinterpreting fragment crystallography.

What would resolve it: Endogenously tag LRFN5 and each LAR-RPTP in paired human neurons, measure direction-resolved proximity and stoichiometry, and test interface- and dimerization-mutant rescue of synaptic structure and transmission.

Provenance (the field's own admissions):

Gap: Whether LRFN5-HVEM signaling suppresses macrophage or microglial activation in human CNS tissue, and which cell type and signaling direction are essential, remain unknown.

OPEN BIOLOGY RESIDUAL_SUBGAP

What is known: Human SALM5 and HVEM bind directly, but the macrophage-coculture and inflammatory disease phenotypes were established in mouse systems. The available evidence does not demonstrate the anti-inflammatory process in human neural tissue or define whether HVEM is the complete macrophage-side signaling mechanism.

Significance: This distinction determines whether the conserved human binding event has the same immunoregulatory consequence and whether it can be separated from LRFN5's synaptic role.

What would resolve it: Use human neuron-microglia or neuron-macrophage cocultures with compartment- specific LRFN5 and TNFRSF14 perturbation, recombinant-interface rescue, cytokine profiling, and single-cell signaling analysis.

Provenance (the field's own admissions):

📚 Additional Documentation

Notes

(LRFN5-notes.md)

Loading supporting content…

Download this section (compressed HTML)

📄 View Raw YAML

Loading supporting content…

Download this section (compressed HTML)