USP8

UniProt ID: P40818
Organism: Homo sapiens
Review Status: IN PROGRESS
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Gene Description

USP8 encodes ubiquitin-specific protease 8/UBPY, a cysteine-type deubiquitinating enzyme that removes ubiquitin from protein substrates, including K48- and K63-linked ubiquitin chains. USP8 acts mainly in cytosolic and endosomal membrane contexts, where it regulates endosomal ubiquitin dynamics, ESCRT-associated cargo sorting, receptor down-regulation, and substrate stability. Somatic activating mutations in the USP8 14-3-3-binding region increase deubiquitinase activity toward EGFR in corticotroph adenomas, linking USP8 to ACTH-producing pituitary adenoma/Cushing disease.

Existing Annotations Review

GO Term Evidence Action Reason
GO:0007032 endosome organization
IBA
GO_REF:0000033
ACCEPT
Summary: USP8 functions at endosomes, regulating endosomal ubiquitin dynamics and receptor/cargo sorting.
Reason: Endosomal localization and endosome organization are well supported by direct USP8/UBPY studies.
Supporting Evidence:
PMID:16520378
localizes to endosomes
PMID:17711858
The UBPY MIT domain is dispensable for its catalytic activity but is essential for its localization to endosomes.
PMID:16520378
UBPY function is essential for growth factor receptor down-regulation
GO:0007265 Ras protein signal transduction
IBA
GO_REF:0000033
KEEP AS NON CORE
Summary: Ras/MAPK signaling is a downstream consequence of receptor turnover regulation and is not USP8 catalytic activity itself.
Reason: USP8 removes ubiquitin from EGFR and can affect downstream MAPK/Ras signaling, but deubiquitination/endosomal sorting is the core function.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Removes conjugated ubiquitin from EGFR thus regulating EGFR degradation and downstream MAPK signaling.
GO:0004843 cysteine-type deubiquitinase activity
IBA
GO_REF:0000033
ACCEPT
Summary: USP8 is a bona fide ubiquitin-specific cysteine deubiquitinase, including activity on K48- and K63-linked ubiquitin chains where tested.
Reason: This is the core molecular function of USP8 and is supported by direct biochemical and cellular evidence.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
file:human/USP8/USP8-uniprot.txt
Converts both 'Lys-48' an 'Lys-63'-linked ubiquitin chains.
GO:0005829 cytosol
IBA
GO_REF:0000033
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0014069 postsynaptic density
IBA
GO_REF:0000033
KEEP AS NON CORE
Summary: Postsynaptic/glutamatergic-synapse annotations are plausible context-specific consequences of USP8 substrate trafficking but are not core gene function.
Reason: Retain as non-core neuronal context; core function remains deubiquitination and endosomal cargo regulation.
Supporting Evidence:
PMID:27302062
regulates the ubiquitination, trafficking, and lysosomal degradation of
GO:0030496 midbody
IBA
GO_REF:0000033
KEEP AS NON CORE
Summary: USP8 has direct evidence for midbody recruitment and cytokinesis defects after depletion, but this is a context-specific role outside the main endosomal deubiquitination function.
Reason: The cytokinesis annotation is supported by PMID:18388320 and should be retained as non-core.
Supporting Evidence:
PMID:18388320
UBPY was detected only in the final stage of cytokinesis at the midbody
PMID:18388320
Depletion of cellular UBPY or AMSH led to defects in cytokinesis.
GO:0004843 cysteine-type deubiquitinase activity
IEA
GO_REF:0000120
ACCEPT
Summary: USP8 is a bona fide ubiquitin-specific cysteine deubiquitinase, including activity on K48- and K63-linked ubiquitin chains where tested.
Reason: This is the core molecular function of USP8 and is supported by direct biochemical and cellular evidence.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
file:human/USP8/USP8-uniprot.txt
Converts both 'Lys-48' an 'Lys-63'-linked ubiquitin chains.
GO:0005634 nucleus
IEA
GO_REF:0000044
KEEP AS NON CORE
Summary: Nuclear localization is weakly supported relative to cytosol/endosome and appears context-dependent.
Reason: Nonmutant corticotroph tumors show cytoplasmic USP8, whereas mutant tumors can show more nuclear staining; this should not be treated as the core normal location.
Supporting Evidence:
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
PMID:28505279
its expression was more nuclear in the mutated tumors
GO:0005737 cytoplasm
IEA
GO_REF:0000044
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0005768 endosome
IEA
GO_REF:0000117
ACCEPT
Summary: USP8 functions at endosomes, regulating endosomal ubiquitin dynamics and receptor/cargo sorting.
Reason: Endosomal localization and endosome organization are well supported by direct USP8/UBPY studies.
Supporting Evidence:
PMID:16520378
localizes to endosomes
PMID:17711858
The UBPY MIT domain is dispensable for its catalytic activity but is essential for its localization to endosomes.
PMID:16520378
UBPY function is essential for growth factor receptor down-regulation
GO:0005886 plasma membrane
IEA
GO_REF:0000044
KEEP AS NON CORE
Summary: USP8 can associate peripherally with cell/endosomal membranes, but this is not the principal location term.
Reason: Retain as non-core localization; endosome membrane/cytosol are more informative for normal USP8 function.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
GO:0010008 endosome membrane
IEA
GO_REF:0000120
ACCEPT
Summary: USP8 functions at endosomes, regulating endosomal ubiquitin dynamics and receptor/cargo sorting.
Reason: Endosomal localization and endosome organization are well supported by direct USP8/UBPY studies.
Supporting Evidence:
PMID:16520378
localizes to endosomes
PMID:17711858
The UBPY MIT domain is dispensable for its catalytic activity but is essential for its localization to endosomes.
PMID:16520378
UBPY function is essential for growth factor receptor down-regulation
GO:0016579 protein deubiquitination
IEA
GO_REF:0000120
ACCEPT
Summary: USP8-mediated protein deubiquitination is central to its regulation of receptor and cargo turnover.
Reason: The process term correctly captures the biological consequence of the USP8 catalytic activity.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
PMID:27302062
USP8 plays a key role in the trafficking and degradation of BACE1 by deubiquitinating lysine 501
GO:0005515 protein binding
IPI
PMID:15161933
Comprehensive proteomic analysis of interphase and mitotic 1...
MARK AS OVER ANNOTATED
Summary: The interaction is retained as context, but generic protein binding is too vague for USP8 functional curation.
Reason: USP8 has many real partners, including CHMP proteins, 14-3-3 proteins, NBR1, RNF41, BIRC6, and KIF23, but the GO term should describe specific binding or the deubiquitination/endosomal process rather than generic protein binding.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Interacts with NBR1, RASGRF1, RNF41 and IST1.
GO:0005515 protein binding
IPI
PMID:15778465
Targeted proteomic analysis of 14-3-3 sigma, a p53 effector ...
MARK AS OVER ANNOTATED
Summary: The interaction is retained as context, but generic protein binding is too vague for USP8 functional curation.
Reason: USP8 has many real partners, including CHMP proteins, 14-3-3 proteins, NBR1, RNF41, BIRC6, and KIF23, but the GO term should describe specific binding or the deubiquitination/endosomal process rather than generic protein binding.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Interacts with NBR1, RASGRF1, RNF41 and IST1.
GO:0005515 protein binding
IPI
PMID:17711858
The MIT domain of UBPY constitutes a CHMP binding and endoso...
MARK AS OVER ANNOTATED
Summary: The interaction is retained as context, but generic protein binding is too vague for USP8 functional curation.
Reason: USP8 has many real partners, including CHMP proteins, 14-3-3 proteins, NBR1, RNF41, BIRC6, and KIF23, but the GO term should describe specific binding or the deubiquitination/endosomal process rather than generic protein binding.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Interacts with NBR1, RASGRF1, RNF41 and IST1.
GO:0005515 protein binding
IPI
PMID:19302785
Ab initio protein modelling reveals novel human MIT domains.
MARK AS OVER ANNOTATED
Summary: The interaction is retained as context, but generic protein binding is too vague for USP8 functional curation.
Reason: USP8 has many real partners, including CHMP proteins, 14-3-3 proteins, NBR1, RNF41, BIRC6, and KIF23, but the GO term should describe specific binding or the deubiquitination/endosomal process rather than generic protein binding.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Interacts with NBR1, RASGRF1, RNF41 and IST1.
GO:0005515 protein binding
IPI
PMID:19427866
Interactions with LC3 and polyubiquitin chains link nbr1 to ...
MARK AS OVER ANNOTATED
Summary: The interaction is retained as context, but generic protein binding is too vague for USP8 functional curation.
Reason: USP8 has many real partners, including CHMP proteins, 14-3-3 proteins, NBR1, RNF41, BIRC6, and KIF23, but the GO term should describe specific binding or the deubiquitination/endosomal process rather than generic protein binding.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Interacts with NBR1, RASGRF1, RNF41 and IST1.
GO:0005515 protein binding
IPI
PMID:24378640
HIF1Ξ± deubiquitination by USP8 is essential for ciliogenesis...
MARK AS OVER ANNOTATED
Summary: The interaction is retained as context, but generic protein binding is too vague for USP8 functional curation.
Reason: USP8 has many real partners, including CHMP proteins, 14-3-3 proteins, NBR1, RNF41, BIRC6, and KIF23, but the GO term should describe specific binding or the deubiquitination/endosomal process rather than generic protein binding.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Interacts with NBR1, RASGRF1, RNF41 and IST1.
GO:0005515 protein binding
IPI
PMID:28514442
Architecture of the human interactome defines protein commun...
MARK AS OVER ANNOTATED
Summary: The interaction is retained as context, but generic protein binding is too vague for USP8 functional curation.
Reason: USP8 has many real partners, including CHMP proteins, 14-3-3 proteins, NBR1, RNF41, BIRC6, and KIF23, but the GO term should describe specific binding or the deubiquitination/endosomal process rather than generic protein binding.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Interacts with NBR1, RASGRF1, RNF41 and IST1.
GO:0005515 protein binding
IPI
PMID:33961781
Dual proteome-scale networks reveal cell-specific remodeling...
MARK AS OVER ANNOTATED
Summary: The interaction is retained as context, but generic protein binding is too vague for USP8 functional curation.
Reason: USP8 has many real partners, including CHMP proteins, 14-3-3 proteins, NBR1, RNF41, BIRC6, and KIF23, but the GO term should describe specific binding or the deubiquitination/endosomal process rather than generic protein binding.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Interacts with NBR1, RASGRF1, RNF41 and IST1.
GO:0005515 protein binding
IPI
PMID:35271311
OpenCell: Endogenous tagging for the cartography of human ce...
MARK AS OVER ANNOTATED
Summary: The interaction is retained as context, but generic protein binding is too vague for USP8 functional curation.
Reason: USP8 has many real partners, including CHMP proteins, 14-3-3 proteins, NBR1, RNF41, BIRC6, and KIF23, but the GO term should describe specific binding or the deubiquitination/endosomal process rather than generic protein binding.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Interacts with NBR1, RASGRF1, RNF41 and IST1.
GO:0005515 protein binding
IPI
PMID:36931259
A central chaperone-like role for 14-3-3 proteins in human c...
MARK AS OVER ANNOTATED
Summary: The interaction is retained as context, but generic protein binding is too vague for USP8 functional curation.
Reason: USP8 has many real partners, including CHMP proteins, 14-3-3 proteins, NBR1, RNF41, BIRC6, and KIF23, but the GO term should describe specific binding or the deubiquitination/endosomal process rather than generic protein binding.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Interacts with NBR1, RASGRF1, RNF41 and IST1.
GO:0002080 acrosomal membrane
IEA
GO_REF:0000107
KEEP AS NON CORE
Summary: Acrosomal membrane localization is a specialized context inferred from orthologous sperm/acrosome biology, not the core human USP8 function.
Reason: UniProt notes acrosome biogenesis through interaction with spermatid ESCRT-0 and microtubules, but the dominant supported function is endosomal deubiquitination.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Involved in acrosome biogenesis through interaction with the spermatid ESCRT-0 complex and microtubules.
GO:0005769 early endosome
IEA
GO_REF:0000107
ACCEPT
Summary: USP8 functions at endosomes, regulating endosomal ubiquitin dynamics and receptor/cargo sorting.
Reason: Endosomal localization and endosome organization are well supported by direct USP8/UBPY studies.
Supporting Evidence:
PMID:16520378
localizes to endosomes
PMID:17711858
The UBPY MIT domain is dispensable for its catalytic activity but is essential for its localization to endosomes.
PMID:16520378
UBPY function is essential for growth factor receptor down-regulation
GO:0005829 cytosol
IEA
GO_REF:0000120
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0007032 endosome organization
IEA
GO_REF:0000107
ACCEPT
Summary: USP8 functions at endosomes, regulating endosomal ubiquitin dynamics and receptor/cargo sorting.
Reason: Endosomal localization and endosome organization are well supported by direct USP8/UBPY studies.
Supporting Evidence:
PMID:16520378
localizes to endosomes
PMID:17711858
The UBPY MIT domain is dispensable for its catalytic activity but is essential for its localization to endosomes.
PMID:16520378
UBPY function is essential for growth factor receptor down-regulation
GO:0014069 postsynaptic density
IEA
GO_REF:0000107
KEEP AS NON CORE
Summary: Postsynaptic/glutamatergic-synapse annotations are plausible context-specific consequences of USP8 substrate trafficking but are not core gene function.
Reason: Retain as non-core neuronal context; core function remains deubiquitination and endosomal cargo regulation.
Supporting Evidence:
PMID:27302062
regulates the ubiquitination, trafficking, and lysosomal degradation of
GO:0030496 midbody
IEA
GO_REF:0000120
KEEP AS NON CORE
Summary: USP8 has direct evidence for midbody recruitment and cytokinesis defects after depletion, but this is a context-specific role outside the main endosomal deubiquitination function.
Reason: The cytokinesis annotation is supported by PMID:18388320 and should be retained as non-core.
Supporting Evidence:
PMID:18388320
UBPY was detected only in the final stage of cytokinesis at the midbody
PMID:18388320
Depletion of cellular UBPY or AMSH led to defects in cytokinesis.
GO:0071549 cellular response to dexamethasone stimulus
IEA
GO_REF:0000107
MARK AS OVER ANNOTATED
Summary: Cellular response to dexamethasone is not a core USP8 function and appears to be a transferred context annotation.
Reason: No direct evidence in the reviewed USP8 sources establishes normal USP8 as a dexamethasone-response effector; disease relevance is through corticotroph EGFR/POMC/ACTH signaling.
Supporting Evidence:
PMID:28505279
decreased EGFR degradation, which in turn leads to increased POMC expression and ACTH production
GO:0098978 glutamatergic synapse
IEA
GO_REF:0000107
KEEP AS NON CORE
Summary: Postsynaptic/glutamatergic-synapse annotations are plausible context-specific consequences of USP8 substrate trafficking but are not core gene function.
Reason: Retain as non-core neuronal context; core function remains deubiquitination and endosomal cargo regulation.
Supporting Evidence:
PMID:27302062
regulates the ubiquitination, trafficking, and lysosomal degradation of
GO:0099576 regulation of protein catabolic process at postsynapse, modulating synaptic transmission
IEA
GO_REF:0000107
KEEP AS NON CORE
Summary: Postsynaptic/glutamatergic-synapse annotations are plausible context-specific consequences of USP8 substrate trafficking but are not core gene function.
Reason: Retain as non-core neuronal context; core function remains deubiquitination and endosomal cargo regulation.
Supporting Evidence:
PMID:27302062
regulates the ubiquitination, trafficking, and lysosomal degradation of
GO:1990090 cellular response to nerve growth factor stimulus
IEA
GO_REF:0000107
KEEP AS NON CORE
Summary: This annotation captures a substrate-specific consequence of USP8 deubiquitination and trafficking regulation.
Reason: The process is true in specific substrate/pathway contexts, but the core function is the upstream deubiquitinase activity and endosomal cargo regulation.
Supporting Evidence:
PMID:27302062
regulates the ubiquitination, trafficking, and lysosomal degradation of
GO:0005829 cytosol
IDA
GO_REF:0000052
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0004843 cysteine-type deubiquitinase activity
TAS
Reactome:R-HSA-4641236
ACCEPT
Summary: USP8 is a bona fide ubiquitin-specific cysteine deubiquitinase, including activity on K48- and K63-linked ubiquitin chains where tested.
Reason: This is the core molecular function of USP8 and is supported by direct biochemical and cellular evidence.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
file:human/USP8/USP8-uniprot.txt
Converts both 'Lys-48' an 'Lys-63'-linked ubiquitin chains.
GO:0004843 cysteine-type deubiquitinase activity
TAS
Reactome:R-HSA-8875443
ACCEPT
Summary: USP8 is a bona fide ubiquitin-specific cysteine deubiquitinase, including activity on K48- and K63-linked ubiquitin chains where tested.
Reason: This is the core molecular function of USP8 and is supported by direct biochemical and cellular evidence.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
file:human/USP8/USP8-uniprot.txt
Converts both 'Lys-48' an 'Lys-63'-linked ubiquitin chains.
GO:0005737 cytoplasm
EXP
PMID:16520378
The ubiquitin isopeptidase UBPY regulates endosomal ubiquiti...
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0005737 cytoplasm
EXP
PMID:17711858
The MIT domain of UBPY constitutes a CHMP binding and endoso...
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0005737 cytoplasm
EXP
PMID:19427866
Interactions with LC3 and polyubiquitin chains link nbr1 to ...
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0005737 cytoplasm
EXP
PMID:28505279
Somatic USP8 Gene Mutations Are a Common Cause of Pediatric ...
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0005886 plasma membrane
EXP
PMID:16520378
The ubiquitin isopeptidase UBPY regulates endosomal ubiquiti...
KEEP AS NON CORE
Summary: USP8 can associate peripherally with cell/endosomal membranes, but this is not the principal location term.
Reason: Retain as non-core localization; endosome membrane/cytosol are more informative for normal USP8 function.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
GO:0010008 endosome membrane
EXP
PMID:16520378
The ubiquitin isopeptidase UBPY regulates endosomal ubiquiti...
ACCEPT
Summary: USP8 functions at endosomes, regulating endosomal ubiquitin dynamics and receptor/cargo sorting.
Reason: Endosomal localization and endosome organization are well supported by direct USP8/UBPY studies.
Supporting Evidence:
PMID:16520378
localizes to endosomes
PMID:17711858
The UBPY MIT domain is dispensable for its catalytic activity but is essential for its localization to endosomes.
PMID:16520378
UBPY function is essential for growth factor receptor down-regulation
GO:0010008 endosome membrane
EXP
PMID:17711858
The MIT domain of UBPY constitutes a CHMP binding and endoso...
ACCEPT
Summary: USP8 functions at endosomes, regulating endosomal ubiquitin dynamics and receptor/cargo sorting.
Reason: Endosomal localization and endosome organization are well supported by direct USP8/UBPY studies.
Supporting Evidence:
PMID:16520378
localizes to endosomes
PMID:17711858
The UBPY MIT domain is dispensable for its catalytic activity but is essential for its localization to endosomes.
PMID:16520378
UBPY function is essential for growth factor receptor down-regulation
GO:0005769 early endosome
IDA
PMID:16520378
The ubiquitin isopeptidase UBPY regulates endosomal ubiquiti...
ACCEPT
Summary: USP8 functions at endosomes, regulating endosomal ubiquitin dynamics and receptor/cargo sorting.
Reason: Endosomal localization and endosome organization are well supported by direct USP8/UBPY studies.
Supporting Evidence:
PMID:16520378
localizes to endosomes
PMID:17711858
The UBPY MIT domain is dispensable for its catalytic activity but is essential for its localization to endosomes.
PMID:16520378
UBPY function is essential for growth factor receptor down-regulation
GO:0005829 cytosol
IDA
PMID:16520378
The ubiquitin isopeptidase UBPY regulates endosomal ubiquiti...
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0061578 K63-linked deubiquitinase activity
IDA
PMID:16520378
The ubiquitin isopeptidase UBPY regulates endosomal ubiquiti...
ACCEPT
Summary: USP8 is a bona fide ubiquitin-specific cysteine deubiquitinase, including activity on K48- and K63-linked ubiquitin chains where tested.
Reason: This is the core molecular function of USP8 and is supported by direct biochemical and cellular evidence.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
file:human/USP8/USP8-uniprot.txt
Converts both 'Lys-48' an 'Lys-63'-linked ubiquitin chains.
GO:1990380 K48-linked deubiquitinase activity
IDA
PMID:16520378
The ubiquitin isopeptidase UBPY regulates endosomal ubiquiti...
ACCEPT
Summary: USP8 is a bona fide ubiquitin-specific cysteine deubiquitinase, including activity on K48- and K63-linked ubiquitin chains where tested.
Reason: This is the core molecular function of USP8 and is supported by direct biochemical and cellular evidence.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
file:human/USP8/USP8-uniprot.txt
Converts both 'Lys-48' an 'Lys-63'-linked ubiquitin chains.
GO:0004843 cysteine-type deubiquitinase activity
IDA
PMID:27444016
Deubiquitinase Usp8 regulates Ξ±-synuclein clearance and modi...
ACCEPT
Summary: USP8 is a bona fide ubiquitin-specific cysteine deubiquitinase, including activity on K48- and K63-linked ubiquitin chains where tested.
Reason: This is the core molecular function of USP8 and is supported by direct biochemical and cellular evidence.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
file:human/USP8/USP8-uniprot.txt
Converts both 'Lys-48' an 'Lys-63'-linked ubiquitin chains.
GO:0005829 cytosol
IDA
PMID:27444016
Deubiquitinase Usp8 regulates Ξ±-synuclein clearance and modi...
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:1905166 negative regulation of lysosomal protein catabolic process
IMP
PMID:27444016
Deubiquitinase Usp8 regulates Ξ±-synuclein clearance and modi...
KEEP AS NON CORE
Summary: This annotation captures a substrate-specific consequence of USP8 deubiquitination and trafficking regulation.
Reason: The process is true in specific substrate/pathway contexts, but the core function is the upstream deubiquitinase activity and endosomal cargo regulation.
Supporting Evidence:
PMID:27302062
regulates the ubiquitination, trafficking, and lysosomal degradation of
GO:1905908 positive regulation of amyloid fibril formation
IMP
PMID:27444016
Deubiquitinase Usp8 regulates Ξ±-synuclein clearance and modi...
MARK AS OVER ANNOTATED
Summary: Positive regulation of amyloid fibril formation is a disease-model consequence of alpha-synuclein deubiquitination, not a core normal function.
Reason: The direct molecular observation is USP8 removal of K63-linked ubiquitin from alpha-synuclein and reduced lysosomal degradation; fibril formation is downstream and pathological.
Supporting Evidence:
PMID:27444016
it deubiquitinated K63-linked chains on alpha-synuclein
PMID:27444016
knockdown increased the lysosomal degradation of alpha-synuclein
GO:0004843 cysteine-type deubiquitinase activity
IDA
PMID:18728397
Usp39 is essential for mitotic spindle checkpoint integrity ...
UNDECIDED
Summary: The cited PMID:18728397 does not support this annotation. The cached publication for PMID:18728397 is "Usp39 is essential for mitotic spindle checkpoint integrity and controls mRNA-levels of aurora B" (van Leuken et al., Cell Cycle 2008), which is about USP39, not USP8. The biological claim (USP8 is a cysteine-type deubiquitinase) is correct and well-supported by other annotations, but this specific GOA entry has an erroneous reference and should be flagged to source curators.
Reason: This specific GOA entry cites PMID:18728397, but the publication is about USP39 (not USP8). The underlying molecular function (GO:0004843) is well-supported by other evidence (e.g., the IBA/IEA annotations and PMID:16520378), so the term itself is correct, but this individual annotation cannot be evaluated against the cited reference. Recommend surfacing the PMID mismatch to the source database curators.
Supporting Evidence:
file:publications/PMID_18728397.md
Usp39 is essential for mitotic spindle checkpoint integrity and controls mRNA-levels of aurora B.
GO:0090263 positive regulation of canonical Wnt signaling pathway
IMP
PMID:20495530
Balanced ubiquitylation and deubiquitylation of Frizzled reg...
KEEP AS NON CORE
Summary: USP8 regulation of Wnt signaling through Frizzled deubiquitination is supported but pathway-specific and non-core.
Reason: PMID:20495530 supports FZD deubiquitination and altered Wnt responsiveness, but this is one substrate/pathway context of the broader deubiquitinase role.
Supporting Evidence:
PMID:20495530
cell surface level of Frizzled is regulated by deubiquitylating enzyme UBPY/ubiquitin-specific protease 8 (USP8)
GO:0016579 protein deubiquitination
IMP
PMID:27302062
The Endosome-associated Deubiquitinating Enzyme USP8 Regulat...
ACCEPT
Summary: USP8-mediated protein deubiquitination is central to its regulation of receptor and cargo turnover.
Reason: The process term correctly captures the biological consequence of the USP8 catalytic activity.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
PMID:27302062
USP8 plays a key role in the trafficking and degradation of BACE1 by deubiquitinating lysine 501
GO:0031647 regulation of protein stability
IMP
PMID:27302062
The Endosome-associated Deubiquitinating Enzyme USP8 Regulat...
KEEP AS NON CORE
Summary: This annotation captures a substrate-specific consequence of USP8 deubiquitination and trafficking regulation.
Reason: The process is true in specific substrate/pathway contexts, but the core function is the upstream deubiquitinase activity and endosomal cargo regulation.
Supporting Evidence:
PMID:27302062
regulates the ubiquitination, trafficking, and lysosomal degradation of
GO:0032880 regulation of protein localization
IMP
PMID:27302062
The Endosome-associated Deubiquitinating Enzyme USP8 Regulat...
KEEP AS NON CORE
Summary: This annotation captures a substrate-specific consequence of USP8 deubiquitination and trafficking regulation.
Reason: The process is true in specific substrate/pathway contexts, but the core function is the upstream deubiquitinase activity and endosomal cargo regulation.
Supporting Evidence:
PMID:27302062
regulates the ubiquitination, trafficking, and lysosomal degradation of
GO:0045296 cadherin binding
HDA
PMID:25468996
E-cadherin interactome complexity and robustness resolved by...
MARK AS OVER ANNOTATED
Summary: Cadherin binding comes from a high-throughput E-cadherin interactome and is not a defining USP8 function.
Reason: The source can be retained as interaction context, but cadherin binding should not be treated as a core molecular function of USP8.
Supporting Evidence:
PMID:25468996
E-cadherin interactome
GO:0005829 cytosol
TAS
Reactome:R-HSA-1358791
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0005829 cytosol
TAS
Reactome:R-HSA-1358795
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0005829 cytosol
TAS
Reactome:R-HSA-1358797
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0005829 cytosol
TAS
Reactome:R-HSA-4641236
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0005829 cytosol
TAS
Reactome:R-HSA-5690196
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0005829 cytosol
TAS
Reactome:R-HSA-6782628
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0005829 cytosol
TAS
Reactome:R-HSA-8875443
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0000281 mitotic cytokinesis
IMP
PMID:18388320
Dynamic regulation of ubiquitylation and deubiquitylation at...
KEEP AS NON CORE
Summary: USP8 has direct evidence for midbody recruitment and cytokinesis defects after depletion, but this is a context-specific role outside the main endosomal deubiquitination function.
Reason: The cytokinesis annotation is supported by PMID:18388320 and should be retained as non-core.
Supporting Evidence:
PMID:18388320
UBPY was detected only in the final stage of cytokinesis at the midbody
PMID:18388320
Depletion of cellular UBPY or AMSH led to defects in cytokinesis.
GO:0004843 cysteine-type deubiquitinase activity
IDA
PMID:18388320
Dynamic regulation of ubiquitylation and deubiquitylation at...
ACCEPT
Summary: USP8 is a bona fide ubiquitin-specific cysteine deubiquitinase, including activity on K48- and K63-linked ubiquitin chains where tested.
Reason: This is the core molecular function of USP8 and is supported by direct biochemical and cellular evidence.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
file:human/USP8/USP8-uniprot.txt
Converts both 'Lys-48' an 'Lys-63'-linked ubiquitin chains.
GO:0005737 cytoplasm
IDA
PMID:18388320
Dynamic regulation of ubiquitylation and deubiquitylation at...
ACCEPT
Summary: Cytosol/cytoplasm localization is consistent with USP8 function as a cytosolic enzyme recruited to endosomal membranes and other cytoplasmic structures.
Reason: The broad cytosolic/cytoplasmic localization is supported by UniProt and direct localization studies.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
CC -!- SUBCELLULAR LOCATION: Cytoplasm {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858, ECO:0000269|PubMed:19427866, CC ECO:0000269|PubMed:28505279}. Nucleus {ECO:0000250|UniProtKB:Q80U87}. CC Endosome membrane {ECO:0000269|PubMed:16520378, CC ECO:0000269|PubMed:17711858}; Peripheral membrane protein CC {ECO:0000305}. Cell membrane {ECO:0000269|PubMed:16520378}; Peripheral CC membrane protein {ECO:0000305}.
PMID:28505279
USP8 was exclusively expressed in the cytoplasm of the nonmutant tumors
GO:0016579 protein deubiquitination
IMP
PMID:18388320
Dynamic regulation of ubiquitylation and deubiquitylation at...
ACCEPT
Summary: USP8-mediated protein deubiquitination is central to its regulation of receptor and cargo turnover.
Reason: The process term correctly captures the biological consequence of the USP8 catalytic activity.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
PMID:27302062
USP8 plays a key role in the trafficking and degradation of BACE1 by deubiquitinating lysine 501
GO:0030496 midbody
IDA
PMID:18388320
Dynamic regulation of ubiquitylation and deubiquitylation at...
KEEP AS NON CORE
Summary: USP8 has direct evidence for midbody recruitment and cytokinesis defects after depletion, but this is a context-specific role outside the main endosomal deubiquitination function.
Reason: The cytokinesis annotation is supported by PMID:18388320 and should be retained as non-core.
Supporting Evidence:
PMID:18388320
UBPY was detected only in the final stage of cytokinesis at the midbody
PMID:18388320
Depletion of cellular UBPY or AMSH led to defects in cytokinesis.
GO:0005515 protein binding
IPI
PMID:18329369
Final stages of cytokinesis and midbody ring formation are c...
MARK AS OVER ANNOTATED
Summary: The interaction is retained as context, but generic protein binding is too vague for USP8 functional curation.
Reason: USP8 has many real partners, including CHMP proteins, 14-3-3 proteins, NBR1, RNF41, BIRC6, and KIF23, but the GO term should describe specific binding or the deubiquitination/endosomal process rather than generic protein binding.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Interacts with NBR1, RASGRF1, RNF41 and IST1.
GO:0004843 cysteine-type deubiquitinase activity
IDA
PMID:16520378
The ubiquitin isopeptidase UBPY regulates endosomal ubiquiti...
ACCEPT
Summary: USP8 is a bona fide ubiquitin-specific cysteine deubiquitinase, including activity on K48- and K63-linked ubiquitin chains where tested.
Reason: This is the core molecular function of USP8 and is supported by direct biochemical and cellular evidence.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
file:human/USP8/USP8-uniprot.txt
Converts both 'Lys-48' an 'Lys-63'-linked ubiquitin chains.
GO:0070536 protein K63-linked deubiquitination
IDA
PMID:16520378
The ubiquitin isopeptidase UBPY regulates endosomal ubiquiti...
ACCEPT
Summary: USP8-mediated protein deubiquitination is central to its regulation of receptor and cargo turnover.
Reason: The process term correctly captures the biological consequence of the USP8 catalytic activity.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
PMID:27302062
USP8 plays a key role in the trafficking and degradation of BACE1 by deubiquitinating lysine 501
GO:0071108 protein K48-linked deubiquitination
IDA
PMID:16520378
The ubiquitin isopeptidase UBPY regulates endosomal ubiquiti...
ACCEPT
Summary: USP8-mediated protein deubiquitination is central to its regulation of receptor and cargo turnover.
Reason: The process term correctly captures the biological consequence of the USP8 catalytic activity.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
PMID:27302062
USP8 plays a key role in the trafficking and degradation of BACE1 by deubiquitinating lysine 501
GO:0004197 cysteine-type endopeptidase activity
TAS
PMID:9827704
Deubiquitinating enzymes: a new class of biological regulato...
MODIFY
Summary: Cysteine-type endopeptidase activity is too broad for USP8; the specific deubiquitinase activity term should be used.
Reason: USP8 is a cysteine protease in the deubiquitinating enzyme family, but GO:0004843 captures the biologically relevant activity.
Supporting Evidence:
PMID:9827704
Deubiquitinating enzymes are cysteine proteases that specifically cleave ubiquitin from ubiquitin-conjugated protein substrates.
GO:0004843 cysteine-type deubiquitinase activity
TAS
PMID:9628861
UBPY: a growth-regulated human ubiquitin isopeptidase.
ACCEPT
Summary: USP8 is a bona fide ubiquitin-specific cysteine deubiquitinase, including activity on K48- and K63-linked ubiquitin chains where tested.
Reason: This is the core molecular function of USP8 and is supported by direct biochemical and cellular evidence.
Supporting Evidence:
file:human/USP8/USP8-uniprot.txt
Hydrolase that can remove conjugated ubiquitin from proteins
PMID:16520378
UBPY is a ubiquitin-specific protease
file:human/USP8/USP8-uniprot.txt
Converts both 'Lys-48' an 'Lys-63'-linked ubiquitin chains.
GO:0005515 protein binding
IPI
PMID:17711858
The MIT domain of UBPY constitutes a CHMP binding and endoso...
KEEP AS NON CORE
Summary: The reported physical interaction is retained as non-core; generic protein binding does not specify the catalytic mechanism.
Reason: Physical interaction and catalytic function are distinct claims. The observed interaction does not independently establish a new enzyme activity.
GO:0005515 protein binding
IPI
PMID:17711858
The MIT domain of UBPY constitutes a CHMP binding and endoso...
KEEP AS NON CORE
Summary: The reported physical interaction is retained as non-core; generic protein binding does not specify the catalytic mechanism.
Reason: Physical interaction and catalytic function are distinct claims. The observed interaction does not independently establish a new enzyme activity.
GO:0005515 protein binding
IPI
PMID:19302785
Ab initio protein modelling reveals novel human MIT domains.
KEEP AS NON CORE
Summary: The reported physical interaction is retained as non-core; generic protein binding does not specify the catalytic mechanism.
Reason: Physical interaction and catalytic function are distinct claims. The observed interaction does not independently establish a new enzyme activity.
GO:0005515 protein binding
IPI
PMID:19302785
Ab initio protein modelling reveals novel human MIT domains.
KEEP AS NON CORE
Summary: The reported physical interaction is retained as non-core; generic protein binding does not specify the catalytic mechanism.
Reason: Physical interaction and catalytic function are distinct claims. The observed interaction does not independently establish a new enzyme activity.
GO:0005515 protein binding
IPI
PMID:24378640
HIF1Ξ± deubiquitination by USP8 is essential for ciliogenesis...
KEEP AS NON CORE
Summary: The reported physical interaction is retained as non-core; generic protein binding does not specify the catalytic mechanism.
Reason: Physical interaction and catalytic function are distinct claims. The observed interaction does not independently establish a new enzyme activity.
GO:0005515 protein binding
IPI
PMID:35271311
OpenCell: Endogenous tagging for the cartography of human ce...
KEEP AS NON CORE
Summary: The reported physical interaction is retained as non-core; generic protein binding does not specify the catalytic mechanism.
Reason: Physical interaction and catalytic function are distinct claims. The observed interaction does not independently establish a new enzyme activity.
GO:0005515 protein binding
IPI
PMID:36931259
A central chaperone-like role for 14-3-3 proteins in human c...
KEEP AS NON CORE
Summary: The reported physical interaction is retained as non-core; generic protein binding does not specify the catalytic mechanism.
Reason: Physical interaction and catalytic function are distinct claims. The observed interaction does not independently establish a new enzyme activity.
GO:0005515 protein binding
IPI
PMID:36931259
A central chaperone-like role for 14-3-3 proteins in human c...
KEEP AS NON CORE
Summary: The reported physical interaction is retained as non-core; generic protein binding does not specify the catalytic mechanism.
Reason: Physical interaction and catalytic function are distinct claims. The observed interaction does not independently establish a new enzyme activity.

Core Functions

USP8 removes ubiquitin from protein substrates, including K48- and K63-linked ubiquitin chains, to regulate endosomal ubiquitin dynamics, receptor/cargo sorting, and substrate stability.

Supporting Evidence:
  • file:human/USP8/USP8-uniprot.txt
    Hydrolase that can remove conjugated ubiquitin from proteins
  • PMID:16520378
    UBPY is a ubiquitin-specific protease
  • PMID:17711858
    The UBPY MIT domain is dispensable for its catalytic activity but is essential for its localization to endosomes.

References

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Suggested Questions for Experts

Q: Which normal pituitary USP8 substrates best explain why activating USP8 mutations drive corticotroph adenoma biology?

Q: Should USP8 substrate-specific pathway annotations be represented as non-core contexts unless direct substrate deubiquitination is shown?

Suggested Experiments

Experiment: Compare ubiquitination, stability, and trafficking of EGFR and other candidate substrates in corticotroph cells expressing wild-type versus PITA4-associated USP8 mutants.

Hypothesis: Activating USP8 mutations will shift substrate ubiquitination and trafficking in corticotroph cells.

Experiment: Map endogenous USP8 interaction/substrate changes at endosomes using catalytic-trap mutants and ubiquitin-remnant proteomics.

Hypothesis: Catalytic-trap and ubiquitin-remnant profiling will distinguish direct USP8 substrates from downstream pathway effects.

Deep Research

Falcon

(USP8-deep-research-falcon.md)

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Manual

(USP8-deep-research-manual.md)

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πŸ“š Additional Documentation

Notes

(USP8-notes.md)

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πŸ“„ View Raw YAML

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