MAN1B1

UniProt ID: Q9UKM7
Organism: Homo sapiens
Review Status: COMPLETE
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Gene Description

MAN1B1 (ER alpha-1,2-mannosidase I, ERManI, ERMan1) is a calcium-dependent, type II single-pass endoplasmic reticulum membrane glycosidase of glycoside hydrolase family 47 (GH47, EC 3.2.1.113) that trims terminal alpha-1,2-linked mannose residues from N-linked oligosaccharides. At low enzyme concentration it removes a single mannose from Man9GlcNAc2 to generate Man8GlcNAc2 isomer B, the first committed mannose-trimming step of N-glycan maturation; at the high local concentrations found in the ER-derived quality control compartment (ERQC) it excises additional alpha-1,2-mannoses to yield Man5-6GlcNAc2. This trimming removes misfolded glycoproteins from the calnexin/reglucosylation folding cycle and generates the demannosylated signal that commits them to ER-associated degradation (ERAD), where the trimmed glycan is recognized by downstream lectins (e.g. OS-9/XTP3-B) and delivered to the HRD1 ubiquitin-ligase machinery. ERManI thus functions as a key "mannose timer" in glycoprotein quality control. It is widely expressed, resides in the ER membrane and concentrates in mobile ER-like quality control vesicles that converge on the pericentriolar ERQC. Biallelic loss-of-function variants cause an autosomal-recessive congenital disorder of glycosylation with intellectual disability (Rafiq syndrome / MAN1B1-CDG).

Existing Annotations Review

GO Term Evidence Action Reason
GO:0016020 membrane
IBA
GO_REF:0000033
MARK AS OVER ANNOTATED
Summary: Generic membrane localization inferred phylogenetically. MAN1B1 is a single-pass type II ER membrane protein, but the more specific endoplasmic reticulum membrane term captures the location informatively.
Reason: Bare "membrane" is uninformative relative to the specific ER membrane annotation; MAN1B1 is anchored in the ER membrane, not membranes generally.
Proposed replacements: endoplasmic reticulum membrane
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane
GO:0005783 endoplasmic reticulum
IBA
GO_REF:0000033
ACCEPT
Summary: MAN1B1 is an ER-resident enzyme; phylogenetic assignment of ER localization is consistent with experimental evidence.
Reason: Correct site of action; MAN1B1 acts in the endoplasmic reticulum on nascent and misfolded glycoproteins.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
IBA
GO_REF:0000033
ACCEPT
Summary: The defining molecular function of MAN1B1; phylogenetic assignment of GH47 alpha-1,2-mannosidase activity is well supported.
Reason: Core molecular function; corroborated by direct enzymatic assays, crystal structures, EC 3.2.1.113, and CAZy GH47 membership.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
Endoplasmic reticulum mannosyl-oligosaccharide 1,2-alpha-mannosidase
GO:0036503 ERAD pathway
IBA
GO_REF:0000033
ACCEPT
Summary: MAN1B1 generates the trimmed-mannose ERAD signal that commits misfolded glycoproteins to degradation; phylogenetic assignment is well supported.
Reason: Core biological process; mannose trimming by ERManI is required for ERAD of misfolded glycoproteins.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
Involved in glycoprotein quality control targeting of misfolded glycoproteins for degradation
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
IEA
GO_REF:0000120
ACCEPT
Summary: Electronic assignment of the core GH47 alpha-1,2-mannosidase activity, consistent with experimental evidence.
Reason: Correct core molecular function; redundant with IDA/EXP evidence.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0005509 calcium ion binding
IEA
GO_REF:0000002
KEEP AS NON CORE
Summary: GH47 mannosidases require a Ca2+ ion in the active site for catalysis; MAN1B1 binds calcium as a structural/catalytic cofactor. This is a real attribute but subsidiary to the mannosidase activity, not an independent calcium-signaling function.
Reason: Accurate structural cofactor requirement of the GH47 fold but not a standalone core function; the catalytic mannosidase activity is the informative function.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
Name=Ca(2+)
PMID:10409699
The mannose cleavage reaction required divalent cations as indicated by inhibition with EDTA or EGTA and reversal of the inhibition by the addition of Ca(2+)
GO:0005789 endoplasmic reticulum membrane
IEA
GO_REF:0000044
ACCEPT
Summary: Electronic transfer of ER membrane localization from the UniProt subcellular location; MAN1B1 is a single-pass type II ER membrane protein.
Reason: Correct compartment; redundant with experimental IDA/EXP ER membrane annotations.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
Single-pass type II membrane protein
GO:0005975 carbohydrate metabolic process
IEA
GO_REF:0000002
MARK AS OVER ANNOTATED
Summary: Generic carbohydrate metabolic process from InterPro; far less informative than the specific N-glycan/mannose trimming and ERAD processes MAN1B1 participates in.
Reason: Over-general; the specific ER mannose trimming (GO:1904380) and ER N-glycan trimming (GO:0140277) terms better capture the biology.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
Endoplasmic reticulum mannosyl-oligosaccharide 1,2-alpha-mannosidase
GO:0009100 glycoprotein metabolic process
IEA
GO_REF:0000117
MARK AS OVER ANNOTATED
Summary: Generic glycoprotein metabolic process from ARBA; correct in essence but far less informative than the specific N-glycan trimming and ERAD annotations.
Reason: Over-general parent process; the specific glycan-trimming/ERAD terms are preferred.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
Involved in glycoprotein quality control targeting of misfolded glycoproteins for degradation
GO:0016020 membrane
IEA
GO_REF:0000002
MARK AS OVER ANNOTATED
Summary: Generic membrane localization from InterPro, superseded by the specific ER membrane annotation.
Reason: Uninformative parent; MAN1B1 is specifically an ER membrane protein.
Proposed replacements: endoplasmic reticulum membrane
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane
GO:0036503 ERAD pathway
IEA
GO_REF:0000117
ACCEPT
Summary: Electronic (ARBA) assignment of the ERAD pathway, consistent with experimental evidence that ERManI mannose trimming is required for ERAD.
Reason: Correct core biological process; redundant with IMP/IDA evidence.
Supporting Evidence:
PMID:18003979
required for trimming to Man 5–6 GlcNAc 2 and for ERAD in cells in vivo
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
TAS
Reactome:R-HSA-4793949
ACCEPT
Summary: Reactome curation of MAN1B1 mannosidase activity (defective-MAN1B1 reaction context).
Reason: Correct core molecular function; redundant with experimental evidence.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
TAS
Reactome:R-HSA-901024
ACCEPT
Summary: Reactome curation of MAN1B1 hydrolysis of a 1,2-linked mannose (a branch).
Reason: Correct core molecular function; redundant with experimental evidence.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
TAS
Reactome:R-HSA-901036
ACCEPT
Summary: Reactome curation of MAN1B1 hydrolysis of a second 1,2-linked mannose (a branch).
Reason: Correct core molecular function; redundant with experimental evidence.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
TAS
Reactome:R-HSA-901039
ACCEPT
Summary: Reactome curation of MAN1B1 hydrolysis of a 1,2-linked mannose (c branch).
Reason: Correct core molecular function; redundant with experimental evidence.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
TAS
Reactome:R-HSA-901074
ACCEPT
Summary: Reactome curation of MAN1B1/EDEM2 hydrolysis of a 1,2-linked mannose (b branch).
Reason: Correct core molecular function; redundant with experimental evidence.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
TAS
Reactome:R-HSA-9036008
ACCEPT
Summary: Reactome curation of MAN1B1 mannosidase activity (defective-MAN1B1 reaction context).
Reason: Correct core molecular function; redundant with experimental evidence.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
TAS
Reactome:R-HSA-9036011
ACCEPT
Summary: Reactome curation of MAN1B1 mannosidase activity (defective-MAN1B1 reaction context).
Reason: Correct core molecular function; redundant with experimental evidence.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
TAS
Reactome:R-HSA-9036012
ACCEPT
Summary: Reactome curation of MAN1B1 mannosidase activity (defective-MAN1B1 reaction context).
Reason: Correct core molecular function; redundant with experimental evidence.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
TAS
Reactome:R-HSA-9696807
ACCEPT
Summary: Reactome curation of MAN1B1 mannosidase activity in the context of N-glycan mannose trimming of viral (SARS-CoV-2) spike.
Reason: Correct core molecular function acting on a viral glycoprotein substrate; redundant with experimental evidence.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0140277 endoplasmic reticulum N-glycan trimming
IMP
PMID:18003979
Endoplasmic reticulum (ER) mannosidase I is compartmentalize...
ACCEPT
Summary: Knockdown/inhibition of ERManI blocks N-glycan trimming in the ER, directly demonstrating its role in ER N-glycan trimming.
Reason: Core biological process with direct experimental (IMP) support.
Supporting Evidence:
PMID:18003979
required for trimming to Man 5–6 GlcNAc 2 and for ERAD in cells in vivo
GO:0036503 ERAD pathway
IDA
PMID:10521544
Cloning and expression of a specific human alpha 1,2-mannosi...
ACCEPT
Summary: MAN1B1 generates the trimmed Man8B glycan that initiates the ERAD-targeting signal during N-glycan maturation.
Reason: Core biological process; ERManI mannose trimming commits misfolded glycoproteins to ERAD.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
Involved in glycoprotein quality control targeting of misfolded glycoproteins for degradation
GO:1904380 endoplasmic reticulum mannose trimming
IDA
PMID:10521544
Cloning and expression of a specific human alpha 1,2-mannosi...
ACCEPT
Summary: The recombinant enzyme directly removes a single alpha-1,2-mannose from Man9GlcNAc to produce Man8GlcNAc isomer B, the first ER mannose-trimming step.
Reason: Core biological process with direct enzymatic (IDA) demonstration of ER mannose trimming.
Supporting Evidence:
PMID:10409699
the enzyme that catalyzes the first mannose trimming step in mammalian Asn-linked oligosaccharide biosynthesis
GO:1904380 endoplasmic reticulum mannose trimming
IMP
PMID:18003979
Endoplasmic reticulum (ER) mannosidase I is compartmentalize...
ACCEPT
Summary: ERManI knockdown impairs ER mannose trimming to Man5-6GlcNAc2 in cells, confirming its role in ER mannose trimming.
Reason: Core biological process with direct experimental (IMP) support.
Supporting Evidence:
PMID:18003979
required for trimming to Man 5–6 GlcNAc 2 and for ERAD in cells in vivo
GO:0005789 endoplasmic reticulum membrane
IDA
PMID:18003979
Endoplasmic reticulum (ER) mannosidase I is compartmentalize...
ACCEPT
Summary: ERManI is localized to the ER membrane and concentrates in the ER-derived quality control compartment.
Reason: Correct compartment with direct experimental support.
Supporting Evidence:
PMID:18003979
ERManI is strikingly concentrated together with the ERAD substrate in the pericentriolar ER-derived quality control compartment
GO:1904380 endoplasmic reticulum mannose trimming
TAS
Reactome:R-HSA-901032
ACCEPT
Summary: Reactome curation of ER mannose trimming in the ER Quality Control Compartment pathway.
Reason: Correct core biological process; redundant with experimental evidence.
Supporting Evidence:
PMID:18003979
required for trimming to Man 5–6 GlcNAc 2 and for ERAD in cells in vivo
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
EXP
PMID:15713668
Mechanism of class 1 (glycosylhydrolase family 47) alpha-man...
ACCEPT
Summary: Structural and kinetic study of the GH47 catalytic mechanism with active-site mutagenesis directly demonstrating the alpha-1,2-mannosidase activity.
Reason: Core molecular function with direct experimental (EXP) and structural support.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0005789 endoplasmic reticulum membrane
EXP
PMID:10409699
Identification, expression, and characterization of a cDNA e...
ACCEPT
Summary: Epitope-tagged ERManI displays an ER pattern of localization in cells, supporting ER membrane localization.
Reason: Correct compartment with experimental support.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
IMP
PMID:18003979
Endoplasmic reticulum (ER) mannosidase I is compartmentalize...
ACCEPT
Summary: Functional knockdown/inhibition experiments tie loss of mannosidase activity to impaired N-glycan trimming, supporting the enables annotation.
Reason: Core molecular function consistent with direct enzymatic assays.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0036503 ERAD pathway
IMP
PMID:18003979
Endoplasmic reticulum (ER) mannosidase I is compartmentalize...
ACCEPT
Summary: ERManI is required for ERAD of a model misfolded glycoprotein in cells; loss leads to accumulation of untrimmed glycans.
Reason: Core biological process with direct experimental (IMP) support.
Supporting Evidence:
PMID:18003979
required for trimming to Man 5–6 GlcNAc 2 and for ERAD in cells in vivo
GO:0036503 ERAD pathway
IMP
PMID:21062743
Mannose trimming is required for delivery of a glycoprotein ...
ACCEPT
Summary: Mannose trimming by ERManI is required for handoff of a substrate glycoprotein from EDEM1 to the late ERAD lectin XTP3-B and the downstream HRD1/SCF(Fbs2) ligases.
Reason: Core biological process; experimentally links ERManI trimming to downstream ERAD steps.
Supporting Evidence:
PMID:21062743
Mannose trimming is required for delivery of a glycoprotein from EDEM1 to XTP3-B
GO:0019082 viral protein processing
TAS
Reactome:R-HSA-9694548
KEEP AS NON CORE
Summary: Reactome annotation of MAN1B1 in N-glycan mannose trimming of the SARS-CoV-2 spike glycoprotein. This is the generic mannosidase activity acting on a viral glycoprotein substrate, not a distinct viral function.
Reason: Real but peripheral; reflects the core mannosidase activity applied to a viral substrate rather than a dedicated viral-processing role.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
EC=3.2.1.113
GO:0036510 trimming of terminal mannose on C branch
TAS
Reactome:R-HSA-901039
ACCEPT
Summary: Reactome curation of the specific sub-step in which ERManI trims the terminal C-branch mannose; an accurate refinement of its trimming activity.
Reason: Correct specific sub-process of N-glycan mannose trimming.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
Endoplasmic reticulum mannosyl-oligosaccharide 1,2-alpha-mannosidase
GO:0031410 cytoplasmic vesicle
IDA
PMID:25411339
Mammalian ER mannosidase I resides in quality control vesicl...
ACCEPT
Summary: At steady state ERManI resides in mobile ER-like quality control vesicles (QCVs) to which ERAD substrates are delivered, supporting a cytoplasmic vesicle localization.
Reason: Genuine localization with direct experimental support (QCVs).
Supporting Evidence:
PMID:25411339
quality control vesicles (QCVs) with ER-like density, to which ERAD substrates are delivered
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
IDA
PMID:10521544
Cloning and expression of a specific human alpha 1,2-mannosi...
ACCEPT
Summary: The recombinant human enzyme directly removes a single alpha-1,2-mannose from Man9GlcNAc to give Man8GlcNAc isomer B, directly demonstrating its mannosidase activity.
Reason: Core molecular function with direct enzymatic (IDA) support.
Supporting Evidence:
PMID:10409699
the enzyme that catalyzes the first mannose trimming step in mammalian Asn-linked oligosaccharide biosynthesis
GO:0044322 endoplasmic reticulum quality control compartment
IDA
PMID:18003979
Endoplasmic reticulum (ER) mannosidase I is compartmentalize...
ACCEPT
Summary: ERManI is strikingly concentrated with ERAD substrate in the pericentriolar ER-derived quality control compartment (ERQC), where its high local concentration enables extensive trimming.
Reason: Genuine, functionally important localization with direct experimental support.
Supporting Evidence:
PMID:18003979
ERManI is strikingly concentrated together with the ERAD substrate in the pericentriolar ER-derived quality control compartment
GO:0044322 endoplasmic reticulum quality control compartment
TAS
PMID:21062743
Mannose trimming is required for delivery of a glycoprotein ...
ACCEPT
Summary: ERQC localization asserted in the context of ERManI-dependent ERAD substrate delivery.
Reason: Consistent with direct IDA evidence for ERQC localization.
Supporting Evidence:
PMID:18003979
pericentriolar ER-derived quality control compartment
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
IDA
PMID:22160784
In vitro mannose trimming property of human ER alpha-1,2 man...
ACCEPT
Summary: In vitro assays show recombinant hERManI generates Man6GlcNAc2 and Man5GlcNAc2 and preferentially trims misfolded glycoproteins, directly demonstrating its mannosidase activity and conformational selectivity.
Reason: Core molecular function with direct in vitro enzymatic (IDA) support.
Supporting Evidence:
PMID:22160784
generated Man(6)GlcNAc(2)-PA and Man(5)GlcNAc(2)-PA from 100 ΞΌM
GO:0005783 endoplasmic reticulum
TAS
PMID:22160784
In vitro mannose trimming property of human ER alpha-1,2 man...
ACCEPT
Summary: ER localization asserted in an in vitro mannose-trimming study; consistent with the established ER residence of ERManI.
Reason: Correct compartment; redundant with experimental ER membrane annotations.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane
GO:0005794 Golgi apparatus
TAS
PMID:22160784
In vitro mannose trimming property of human ER alpha-1,2 man...
KEEP AS NON CORE
Summary: A Golgi localization has been reported for ERManI, but later work attributes the apparent Golgi pattern to membrane disturbance during immunofluorescence; ERManI functions in the ER/ERQC, not the Golgi.
Reason: Disputed/likely fixation artifact; not a genuine site of action. Retained as non-core rather than removed because a TAS source asserts it.
Supporting Evidence:
PMID:25411339
Golgi pattern
GO:1903561 extracellular vesicle
HDA
PMID:24769233
Proteomic analysis of cerebrospinal fluid extracellular vesi...
KEEP AS NON CORE
Summary: High-throughput proteomic detection of MAN1B1 in cerebrospinal fluid extracellular vesicles; a real but peripheral detection unrelated to its ER catalytic function.
Reason: Large-scale proteomics detection; not a functional site of action.
Supporting Evidence:
PMID:24769233
cerebrospinal fluid
GO:0044322 endoplasmic reticulum quality control compartment
TAS
Reactome:R-HSA-4793949
ACCEPT
Summary: Reactome curation of ERQC localization (defective-MAN1B1 reaction context).
Reason: Correct compartment; redundant with IDA ERQC evidence.
Supporting Evidence:
PMID:18003979
pericentriolar ER-derived quality control compartment
GO:0044322 endoplasmic reticulum quality control compartment
TAS
Reactome:R-HSA-9036008
ACCEPT
Summary: Reactome curation of ERQC localization (defective-MAN1B1 reaction context).
Reason: Correct compartment; redundant with IDA ERQC evidence.
Supporting Evidence:
PMID:18003979
pericentriolar ER-derived quality control compartment
GO:0044322 endoplasmic reticulum quality control compartment
TAS
Reactome:R-HSA-9036011
ACCEPT
Summary: Reactome curation of ERQC localization (defective-MAN1B1 reaction context).
Reason: Correct compartment; redundant with IDA ERQC evidence.
Supporting Evidence:
PMID:18003979
pericentriolar ER-derived quality control compartment
GO:0044322 endoplasmic reticulum quality control compartment
TAS
Reactome:R-HSA-9036012
ACCEPT
Summary: Reactome curation of ERQC localization (defective-MAN1B1 reaction context).
Reason: Correct compartment; redundant with IDA ERQC evidence.
Supporting Evidence:
PMID:18003979
pericentriolar ER-derived quality control compartment
GO:0016020 membrane
HDA
PMID:19946888
Defining the membrane proteome of NK cells.
MARK AS OVER ANNOTATED
Summary: High-throughput membrane proteome detection of MAN1B1; consistent with its membrane anchoring but uninformative relative to the specific ER membrane term.
Reason: Generic membrane term from proteomics; MAN1B1 is specifically an ER membrane protein.
Proposed replacements: endoplasmic reticulum membrane
Supporting Evidence:
PMID:19946888
membrane proteome
GO:0044322 endoplasmic reticulum quality control compartment
TAS
Reactome:R-HSA-901024
ACCEPT
Summary: Reactome curation of ERQC localization.
Reason: Correct compartment; redundant with IDA ERQC evidence.
Supporting Evidence:
PMID:18003979
pericentriolar ER-derived quality control compartment
GO:0044322 endoplasmic reticulum quality control compartment
TAS
Reactome:R-HSA-901036
ACCEPT
Summary: Reactome curation of ERQC localization.
Reason: Correct compartment; redundant with IDA ERQC evidence.
Supporting Evidence:
PMID:18003979
pericentriolar ER-derived quality control compartment
GO:0044322 endoplasmic reticulum quality control compartment
TAS
Reactome:R-HSA-901039
ACCEPT
Summary: Reactome curation of ERQC localization.
Reason: Correct compartment; redundant with IDA ERQC evidence.
Supporting Evidence:
PMID:18003979
pericentriolar ER-derived quality control compartment
GO:0044322 endoplasmic reticulum quality control compartment
TAS
Reactome:R-HSA-901074
ACCEPT
Summary: Reactome curation of ERQC localization.
Reason: Correct compartment; redundant with IDA ERQC evidence.
Supporting Evidence:
PMID:18003979
pericentriolar ER-derived quality control compartment
GO:0044322 endoplasmic reticulum quality control compartment
TAS
Reactome:R-HSA-9696807
ACCEPT
Summary: Reactome curation of ERQC localization in the spike N-glycan trimming pathway.
Reason: Correct compartment; redundant with IDA ERQC evidence.
Supporting Evidence:
PMID:18003979
pericentriolar ER-derived quality control compartment
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
IDA
PMID:12090241
The specificity of the yeast and human class I ER alpha 1,2-...
ACCEPT
Summary: Demonstrates that the human class I ER alpha-1,2-mannosidase can trim beyond a single mannose, refining the specificity of the mannosidase activity.
Reason: Core molecular function with direct experimental support; informs the broader-than-single-residue specificity underlying the mannose timer.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
at high enzyme concentrations, as found in the ER
GO:0005783 endoplasmic reticulum
IDA
PMID:18003979
Endoplasmic reticulum (ER) mannosidase I is compartmentalize...
ACCEPT
Summary: Direct evidence for ER localization of ERManI.
Reason: Correct site of action with direct experimental support.
Supporting Evidence:
PMID:18003979
pericentriolar ER-derived quality control compartment
GO:0016020 membrane
IDA
PMID:18003979
Endoplasmic reticulum (ER) mannosidase I is compartmentalize...
MARK AS OVER ANNOTATED
Summary: Generic membrane localization; superseded by the specific ER membrane annotation from the same evidence.
Reason: Uninformative parent of the specific ER membrane localization.
Proposed replacements: endoplasmic reticulum membrane
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
TAS
PMID:10409699
Identification, expression, and characterization of a cDNA e...
ACCEPT
Summary: Identification and characterization of human ER mannosidase I as the enzyme catalyzing the first mannose-trimming step.
Reason: Core molecular function with strong experimental basis.
Supporting Evidence:
PMID:10409699
the enzyme that catalyzes the first mannose trimming step in mammalian Asn-linked oligosaccharide biosynthesis
GO:0005783 endoplasmic reticulum
TAS
PMID:10409699
Identification, expression, and characterization of a cDNA e...
ACCEPT
Summary: ER localization asserted from the original characterization of ER mannosidase I.
Reason: Correct site of action; consistent with experimental ER membrane evidence.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane
GO:0009311 oligosaccharide metabolic process
TAS
PMID:10409699
Identification, expression, and characterization of a cDNA e...
MARK AS OVER ANNOTATED
Summary: Generic oligosaccharide metabolic process; correct but far less informative than the specific N-glycan/mannose trimming terms.
Reason: Over-general parent process; the specific ER mannose trimming term is preferred.
Supporting Evidence:
PMID:10409699
Asn-linked oligosaccharide biosynthesis
GO:0004571 mannosyl-oligosaccharide 1,2-alpha-mannosidase activity
TAS
PMID:10521544
Cloning and expression of a specific human alpha 1,2-mannosi...
ACCEPT
Summary: Original cloning/characterization establishing the specific human alpha-1,2-mannosidase activity producing Man8GlcNAc2 isomer B.
Reason: Core molecular function with strong experimental basis.
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
Endoplasmic reticulum mannosyl-oligosaccharide 1,2-alpha-mannosidase
GO:0005509 calcium ion binding
TAS
PMID:10521544
Cloning and expression of a specific human alpha 1,2-mannosi...
KEEP AS NON CORE
Summary: Calcium is required for ERManI activity; this is a structural/catalytic cofactor requirement of the GH47 fold rather than an independent calcium-signaling function.
Reason: Real cofactor requirement but subsidiary to the catalytic mannosidase activity.
Supporting Evidence:
PMID:10521544
Calcium is required for enzyme activity
GO:0016020 membrane
TAS
PMID:10521544
Cloning and expression of a specific human alpha 1,2-mannosi...
MARK AS OVER ANNOTATED
Summary: Generic membrane localization; superseded by the specific ER membrane annotation.
Reason: Uninformative parent; MAN1B1 is specifically an ER membrane protein.
Proposed replacements: endoplasmic reticulum membrane
Supporting Evidence:
file:human/MAN1B1/MAN1B1-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane

Core Functions

Endoplasmic reticulum membrane-anchored alpha-1,2-mannosidase that hydrolyzes terminal alpha-1,2-linked mannose residues from N-linked oligosaccharides, generating Man8GlcNAc2 isomer B and, at high local concentration, Man5-6GlcNAc2.

Supporting Evidence:
  • PMID:10409699
    the enzyme that catalyzes the first mannose trimming step in mammalian Asn-linked oligosaccharide biosynthesis
  • file:human/MAN1B1/MAN1B1-uniprot.txt
    Endoplasmic reticulum mannosyl-oligosaccharide 1,2-alpha-mannosidase

Quality-control "mannose timer" that, by trimming N-glycans on misfolded glycoproteins in the ER/ERQC, removes them from the calnexin folding cycle and generates the demannosylated signal that commits them to ER-associated degradation.

Supporting Evidence:
  • PMID:18003979
    required for trimming to Man 5–6 GlcNAc 2 and for ERAD in cells in vivo
  • PMID:21062743
    Mannose trimming is required for delivery of a glycoprotein from EDEM1 to XTP3-B

References

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Suggested Questions for Experts

Q: What determines the conformational selectivity by which ERManI preferentially trims mannoses from misfolded versus correctly folded glycoproteins, and is this intrinsic to the enzyme or dependent on ERQC cofactors?

Q: How is the high local concentration of ERManI in quality control vesicles/ERQC regulated to tune the kinetics of the mannose timer?

Suggested Experiments

Experiment: Reconstitute ERManI trimming on defined folded versus misfolded glycoprotein substrates at controlled enzyme concentrations to quantify how local concentration and substrate conformation set the rate of progression from Man9 to Man5-6.

Experiment: Live-cell imaging of QCV/ERQC dynamics in cells expressing wild-type versus Rafiq-syndrome (R334C, E397K) MAN1B1 variants to test how disease mutations affect localization, vesicle trafficking, and ERAD substrate clearance.

Deep Research

Falcon

(MAN1B1-deep-research-falcon.md)

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πŸ“š Additional Documentation

Notes

(MAN1B1-notes.md)

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Pn Notes

(MAN1B1-pn-notes.md)

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πŸ“„ View Raw YAML

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