CCDC47

UniProt ID: Q96A33
Organism: Homo sapiens
Review Status: COMPLETE
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Gene Description

CCDC47 (also called calumin) is a widely conserved, single-pass type I endoplasmic reticulum membrane protein with a small cytosolic domain, a single transmembrane helix, and a large luminal domain ending in a disordered, basic, coiled-coil region. It is the scaffold subunit of the PAT (protein associated with the ER translocon) complex, an obligate heterodimer with WDR83OS/Asterix. The PAT complex is one of three accessory subcomplexes (GEL, BOS, PAT) of the ribosome-associated multi-pass translocon (MPT) that assembles around the Sec61 channel during synthesis of multi-pass membrane proteins. Within this assembly CCDC47 occludes the lateral gate of Sec61 and stabilizes Asterix, which directly engages and shields hydrophilic transmembrane segments of nascent multi-pass clients until they fold, thereby promoting the biogenesis of GPCRs, channels, transporters and other polytopic membrane proteins. CCDC47 binds Ca2+ with low affinity and high capacity and contributes to ER calcium storage and signaling, and it has been linked to ER-associated degradation (ERAD) and to maintenance of ER organization during embryogenesis. Biallelic loss-of-function variants cause an autosomal recessive trichohepatoneurodevelopmental syndrome (woolly hair, liver dysfunction, dysmorphic features, hypotonia, developmental delay).

Existing Annotations Review

GO Term Evidence Action Reason
GO:0005783 endoplasmic reticulum
IBA
GO_REF:0000033
ACCEPT
Summary: ER localization is well supported and is the compartment where CCDC47 performs its core membrane-biogenesis scaffold function.
Reason: CCDC47 is an ER-resident membrane protein, directly demonstrated by multiple experimental studies; ER residence is required for its role in the multi-pass translocon.
Supporting Evidence:
file:human/CCDC47/CCDC47-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane
PMID:32814900
CCDC47 is an ER-resident single-pass membrane protein with a well-conserved cytosolic domain
GO:0005509 calcium ion binding
IBA
GO_REF:0000033
KEEP AS NON CORE
Summary: CCDC47/calumin binds calcium with low affinity and high capacity, consistent with an ER calcium-buffering property, but this is secondary to its membrane-biogenesis role.
Reason: Calcium binding is a genuine biochemical property supporting ER calcium storage, but the central, conserved function of CCDC47 is as the PAT/MPT scaffold; retain as non-core.
Supporting Evidence:
PMID:30401460
CCDC47, also known as calumin, has been shown to bind Ca2+ with low affinity and high capacity.
GO:0005509 calcium ion binding
IEA
GO_REF:0000120
KEEP AS NON CORE
Summary: Automated transfer of calcium ion binding agrees with experimental low-affinity, high-capacity Ca2+ binding by CCDC47/calumin.
Reason: Consistent with experimental evidence; retained as non-core relative to the membrane-biogenesis scaffold function.
Supporting Evidence:
PMID:30401460
CCDC47, also known as calumin, has been shown to bind Ca2+ with low affinity and high capacity.
GO:0005783 endoplasmic reticulum
IEA
GO_REF:0000120
ACCEPT
Summary: Automated ER localization is consistent with direct experimental evidence.
Reason: ER residence is well established and is core to CCDC47 function.
Supporting Evidence:
file:human/CCDC47/CCDC47-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane
GO:0005789 endoplasmic reticulum membrane
IEA
GO_REF:0000044
ACCEPT
Summary: ER membrane localization is the precise, well-supported compartment for this single-pass type I membrane protein.
Reason: Direct experimental and structural evidence place CCDC47 in the ER membrane as part of the translocon; this is the correct specific localization term.
Supporting Evidence:
file:human/CCDC47/CCDC47-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane
PMID:32814900
CCDC47 is an ER-resident single-pass membrane protein with a well-conserved cytosolic domain
GO:0006457 protein folding
IEA
GO_REF:0000108
MODIFY
Summary: Generic protein folding understates CCDC47's specific role; the PAT/MPT function is membrane protein biogenesis/insertion, best captured by the specific multi-pass insertion term.
Reason: CCDC47 acts as an intramembrane chaperone in multi-pass membrane protein biogenesis rather than in generic (soluble) protein folding; replace with the specific process term.
Supporting Evidence:
PMID:32814900
Thus, the PAT complex is an intramembrane chaperone that protects TMDs during assembly to minimize misfolding of multi-spanning membrane proteins and maintain cellular protein homeostasis.
GO:0030867 rough endoplasmic reticulum membrane
IEA
GO_REF:0000044
ACCEPT
Summary: Rough ER membrane is consistent with CCDC47 being a ribosome-associated translocon component.
Reason: CCDC47 is part of a ribosome-bound (rough ER) translocon assembly; the rough ER membrane localization is appropriate.
Supporting Evidence:
file:human/CCDC47/CCDC47-uniprot.txt
Rough endoplasmic reticulum membrane
GO:0032469 endoplasmic reticulum calcium ion homeostasis
IEA
GO_REF:0000002
KEEP AS NON CORE
Summary: ER calcium homeostasis is supported by patient-cell data showing reduced ER calcium stores, but is secondary to the biogenesis scaffold function.
Reason: Loss-of-function patient cells show decreased ER Ca2+ storage and impaired Ca2+ signaling, supporting a role in ER calcium homeostasis; retain as a non-core contextual function.
Supporting Evidence:
PMID:30401460
In vitro cellular experiments showed decreased total ER Ca2+ storage, impaired Ca2+ signaling mediated by the IP3R Ca2+ release channel, and reduced ER Ca2+ refilling via store-operated Ca2+ entry.
GO:0005515 protein binding
IPI
PMID:21903422
Mapping a dynamic innate immunity protein interaction networ...
MARK AS OVER ANNOTATED
Summary: Generic protein binding from an innate-immunity interaction network is uninformative for CCDC47 function.
Reason: Bare protein binding from a high-throughput interactome does not capture a physiologically interpretable CCDC47 function.
GO:0005515 protein binding
IPI
PMID:32814053
Interactome Mapping Provides a Network of Neurodegenerative ...
MARK AS OVER ANNOTATED
Summary: Generic protein binding from a neurodegenerative-disease interactome map is uninformative.
Reason: High-throughput protein binding does not identify a specific CCDC47 molecular function.
GO:0005515 protein binding
IPI
PMID:32814900
An intramembrane chaperone complex facilitates membrane prot...
MARK AS OVER ANNOTATED
Summary: The meaningful interaction underlying this annotation is the obligate CCDC47-Asterix (WDR83OS) PAT complex, which is captured by the complex/chaperone terms; bare protein binding is uninformative.
Reason: The specific WDR83OS/Asterix interaction is better represented by the PAT complex (protein folding chaperone complex / multi-pass translocon complex) and chaperone annotations than by generic protein binding.
Supporting Evidence:
PMID:32814900
CCDC47 and Asterix form an obligate complex because knockdown or knockout of either protein results in substantial loss of the other
GO:0005515 protein binding
IPI
PMID:35271311
OpenCell: Endogenous tagging for the cartography of human ce...
MARK AS OVER ANNOTATED
Summary: Generic protein binding from the OpenCell endogenous-tagging interactome/localization cartography is uninformative.
Reason: High-throughput protein binding does not capture a specific CCDC47 function.
GO:0005791 rough endoplasmic reticulum
IEA
GO_REF:0000107
ACCEPT
Summary: Rough ER localization is consistent with CCDC47 being a ribosome-associated translocon factor.
Reason: Consistent with the membrane-protein-biogenesis role at the ribosome-Sec61 channel of the rough ER.
Supporting Evidence:
file:human/CCDC47/CCDC47-uniprot.txt
Rough endoplasmic reticulum membrane
GO:0005783 endoplasmic reticulum
IDA
GO_REF:0000052
ACCEPT
Summary: Immunofluorescence-based ER annotation is consistent with the established ER residence of CCDC47.
Reason: Direct localization evidence supports ER residence, the core compartment for CCDC47.
Supporting Evidence:
file:human/CCDC47/CCDC47-uniprot.txt
SUBCELLULAR LOCATION: Endoplasmic reticulum membrane
GO:0005789 endoplasmic reticulum membrane
IDA
PMID:32814900
An intramembrane chaperone complex facilitates membrane prot...
ACCEPT
Summary: Direct evidence places CCDC47 in the ER membrane as a single-pass component of the PAT complex.
Reason: The PAT-complex study directly demonstrates CCDC47 as an ER membrane protein; this is the correct specific localization.
Supporting Evidence:
PMID:32814900
CCDC47 is an ER-resident single-pass membrane protein with a well-conserved cytosolic domain
GO:0045048 protein insertion into ER membrane
IDA
PMID:32814900
An intramembrane chaperone complex facilitates membrane prot...
MODIFY
Summary: CCDC47 promotes biogenesis of multi-spanning membrane proteins as part of the PAT complex; the more specific multi-pass insertion term better captures this.
Reason: The general ER protein-insertion term is correct but imprecise; CCDC47 acts specifically in multi-pass (polytopic) membrane protein insertion/biogenesis.
Supporting Evidence:
PMID:32814900
Cells that lack either subunit of the PAT complex show reduced biogenesis of
PMID:32814900
Thus, the PAT complex is an intramembrane chaperone that protects TMDs during assembly to minimize misfolding of multi-spanning membrane proteins and maintain cellular protein homeostasis.
GO:0101031 protein folding chaperone complex
IPI
PMID:32814900
An intramembrane chaperone complex facilitates membrane prot...
ACCEPT
Summary: CCDC47 is part of the PAT intramembrane chaperone complex, captured well by this term.
Reason: The obligate CCDC47-Asterix PAT complex functions as an intramembrane chaperone; this complex annotation is directly supported.
Supporting Evidence:
PMID:32814900
Here we identify the PAT complex, an abundant obligate heterodimer of the widely conserved ER-resident membrane proteins CCDC47 and Asterix.
PMID:32814900
Thus, the PAT complex is an intramembrane chaperone that protects TMDs during assembly to minimize misfolding of multi-spanning membrane proteins and maintain cellular protein homeostasis.
GO:0160064 multi-pass translocon complex
IPI
PMID:36261522
Substrate-driven assembly of a translocon for multipass memb...
ACCEPT
Summary: CCDC47 (within the PAT subcomplex) is a component of the multi-pass translocon; this is the most specific and accurate complex term.
Reason: The multi-pass translocon study directly establishes the PAT complex (CCDC47/Asterix) as one of three accessory subcomplexes of the MPT.
Supporting Evidence:
PMID:36261522
This 'multipass translocon' is distinguished by three components that selectively bind the ribosome-Sec61 complex during multipass protein synthesis: the GET- and EMC-like (GEL), protein associated with translocon (PAT) and back of Sec61 (BOS) complexes.
GO:0005789 endoplasmic reticulum membrane
EXP
PMID:25009997
Contribution of calumin to embryogenesis through participati...
ACCEPT
Summary: Experimental evidence supports ER membrane localization of CCDC47/calumin.
Reason: Consistent with established ER membrane residence.
Supporting Evidence:
PMID:25009997
Calumin is an endoplasmic reticulum (ER)-transmembrane protein
GO:0005789 endoplasmic reticulum membrane
EXP
PMID:30401460
Bi-allelic CCDC47 Variants Cause a Disorder Characterized by...
ACCEPT
Summary: Experimental evidence supports ER membrane localization of CCDC47/calumin.
Reason: Consistent with established ER membrane residence; this is the core compartment.
Supporting Evidence:
PMID:30401460
bi-allelic variants in CCDC47 that encodes the Ca2+-binding ER transmembrane protein CCDC47
GO:0030867 rough endoplasmic reticulum membrane
ISS
GO_REF:0000024
ACCEPT
Summary: Orthology-based rough ER membrane localization is consistent with the ribosome-associated translocon role.
Reason: Consistent with experimental ER membrane localization and ribosome association.
Supporting Evidence:
file:human/CCDC47/CCDC47-uniprot.txt
Rough endoplasmic reticulum membrane
GO:0160063 multi-pass transmembrane protein insertion into ER membrane
IDA
PMID:36261522
Substrate-driven assembly of a translocon for multipass memb...
ACCEPT
Summary: This is the most precise core biological process for CCDC47 - facilitating insertion/biogenesis of multi-pass membrane proteins via the multi-pass translocon.
Reason: Directly supported by reconstitution and depletion studies showing the multi-pass translocon components (including CCDC47/PAT) are required for multi-pass protein topogenesis and stability.
Supporting Evidence:
PMID:36261522
Reconstitution studies demonstrate a role for multipass translocon components in protein topogenesis, and cells lacking these components show reduced multipass protein stability.
GO:0160064 multi-pass translocon complex
IDA
PMID:36261522
Substrate-driven assembly of a translocon for multipass memb...
ACCEPT
Summary: Direct structural/biochemical evidence places CCDC47 (PAT subcomplex) in the multi-pass translocon.
Reason: The most specific and accurate complex localization for CCDC47, directly demonstrated.
Supporting Evidence:
PMID:36261522
This 'multipass translocon' is distinguished by three components that selectively bind the ribosome-Sec61 complex during multipass protein synthesis: the GET- and EMC-like (GEL), protein associated with translocon (PAT) and back of Sec61 (BOS) complexes.
GO:0005515 protein binding
IPI
PMID:32820719
An ER translocon for multi-pass membrane protein biogenesis.
MARK AS OVER ANNOTATED
Summary: The meaningful interactions underlying this annotation are CCDC47's associations within the Sec61/MPT translocon; bare protein binding is uninformative.
Reason: The specific translocon interactions are captured by the multi-pass translocon complex annotation; generic protein binding adds nothing.
Supporting Evidence:
PMID:32820719
Here we describe a ~ 360 kDa ribosome-associated complex comprising the core Sec61 channel and five accessory factors: TMCO1, CCDC47 and the Nicalin-TMEM147-NOMO complex.
GO:0043022 ribosome binding
IDA
PMID:32820719
An ER translocon for multi-pass membrane protein biogenesis.
ACCEPT
Summary: CCDC47 is part of a ribosome-associated translocon assembly, supporting a ribosome-binding molecular function.
Reason: Cryo-EM and biochemistry place CCDC47 within a ribosome-associated Sec61 translocon complex; ribosome binding is supported and relevant to co-translational multi-pass biogenesis.
Supporting Evidence:
PMID:32820719
Here we describe a ~ 360 kDa ribosome-associated complex comprising the core Sec61 channel and five accessory factors: TMCO1, CCDC47 and the Nicalin-TMEM147-NOMO complex.
GO:0044183 protein folding chaperone
IDA
PMID:32814900
An intramembrane chaperone complex facilitates membrane prot...
ACCEPT
Summary: As part of the PAT intramembrane chaperone, CCDC47 contributes chaperone activity that protects nascent transmembrane domains during multi-pass biogenesis.
Reason: The PAT complex is directly described as an intramembrane chaperone; CCDC47 is its scaffold/occluder subunit. Note Asterix is the substrate-contacting subunit, but the chaperone-function annotation at the protein level is appropriate.
Supporting Evidence:
PMID:32814900
Thus, the PAT complex is an intramembrane chaperone that protects TMDs during assembly to minimize misfolding of multi-spanning membrane proteins and maintain cellular protein homeostasis.
GO:0032469 endoplasmic reticulum calcium ion homeostasis
IMP
PMID:30401460
Bi-allelic CCDC47 Variants Cause a Disorder Characterized by...
KEEP AS NON CORE
Summary: Patient-cell loss-of-function data directly support a role for CCDC47 in ER calcium homeostasis, but this is a secondary/contextual function.
Reason: Reduced ER Ca2+ storage and impaired Ca2+ signaling in CCDC47-deficient cells support this process; retain as non-core relative to the membrane-biogenesis scaffold role.
Supporting Evidence:
PMID:30401460
In vitro cellular experiments showed decreased total ER Ca2+ storage, impaired Ca2+ signaling mediated by the IP3R Ca2+ release channel, and reduced ER Ca2+ refilling via store-operated Ca2+ entry.
GO:0036503 ERAD pathway
IMP
PMID:25009997
Contribution of calumin to embryogenesis through participati...
KEEP AS NON CORE
Summary: Calumin co-IPs with ERAD machinery and its knockdown reduces ERAD efficiency, supporting involvement in ER-associated degradation as a secondary function.
Reason: Experimental knockdown data link CCDC47/calumin to ERAD efficiency, but this is a contextual ER proteostasis role distinct from its core multi-pass biogenesis scaffold function.
Supporting Evidence:
PMID:25009997
calumin knockdown in HEK 293 cells resulted in ERAD being less efficient, as demonstrated by attenuation in both degradations of a misfolded Ξ±1-antitrypsin variant and the ER-to-cytosol dislocation of cholera toxin A1 subunit.
GO:0001649 osteoblast differentiation
HDA
PMID:16210410
Differential expression profiling of membrane proteins by qu...
MARK AS OVER ANNOTATED
Summary: This annotation derives from detection of CCDC47 in a differential membrane-proteomics dataset of an MSC line during osteoblast differentiation, not from functional evidence.
Reason: Presence in a high-throughput differential proteomics profile is not evidence that CCDC47 functions in osteoblast differentiation.
Supporting Evidence:
PMID:16210410
we used MS to characterize changes in expression of membrane protein markers before and after short-term induction of osteoblast (OB) differentiation
GO:0016020 membrane
HDA
PMID:16210410
Differential expression profiling of membrane proteins by qu...
MARK AS OVER ANNOTATED
Summary: Generic membrane localization is subsumed by the specific ER membrane annotations.
Reason: The bare membrane term is uninformative given direct, specific ER membrane localization evidence.
GO:0016020 membrane
HDA
PMID:19946888
Defining the membrane proteome of NK cells.
MARK AS OVER ANNOTATED
Summary: Generic membrane localization from an NK-cell membrane-proteome dataset is uninformative.
Reason: Subsumed by the specific ER membrane localization; bare membrane adds nothing.
GO:0003723 RNA binding
HDA
PMID:22658674
Insights into RNA biology from an atlas of mammalian mRNA-bi...
MARK AS OVER ANNOTATED
Summary: This annotation comes from a high-throughput mRNA interactome-capture atlas; there is no specific evidence of a physiological RNA-binding function for CCDC47.
Reason: High-throughput crosslinking capture does not establish a meaningful RNA-binding molecular function for an ER membrane translocon scaffold.
Supporting Evidence:
PMID:22658674
Employing two complementary protocols for covalent UV crosslinking of RBPs to RNA, we describe a systematic, unbiased, and comprehensive approach, termed "interactome capture," to define the mRNA interactome of proliferating human HeLa cells.

Core Functions

CCDC47 is the scaffold subunit of the PAT intramembrane chaperone complex (an obligate heterodimer with WDR83OS/Asterix), a component of the ribosome-associated multi-pass translocon that promotes biogenesis of multi-pass (polytopic) membrane proteins downstream of Sec61. CCDC47 occludes the Sec61 lateral gate and stabilizes Asterix, which shields hydrophilic transmembrane segments of nascent clients until they fold.

Supporting Evidence:
  • PMID:32814900
    Here we identify the PAT complex, an abundant obligate heterodimer of the widely conserved ER-resident membrane proteins CCDC47 and Asterix.
  • PMID:32814900
    Thus, the PAT complex is an intramembrane chaperone that protects TMDs during assembly to minimize misfolding of multi-spanning membrane proteins and maintain cellular protein homeostasis.
  • PMID:36261522
    Reconstitution studies demonstrate a role for multipass translocon components in protein topogenesis, and cells lacking these components show reduced multipass protein stability.

CCDC47/calumin contributes to ER calcium homeostasis as a low-affinity, high-capacity Ca2+-binding ER membrane protein; loss of function reduces ER calcium stores and impairs ER calcium signaling.

Supporting Evidence:
  • PMID:30401460
    CCDC47, also known as calumin, has been shown to bind Ca2+ with low affinity and high capacity.
  • PMID:30401460
    In vitro cellular experiments showed decreased total ER Ca2+ storage, impaired Ca2+ signaling mediated by the IP3R Ca2+ release channel, and reduced ER Ca2+ refilling via store-operated Ca2+ entry.

References

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Suggested Questions for Experts

Q: Does CCDC47 contribute catalytically/mechanistically to multi-pass biogenesis beyond stabilizing Asterix and occluding the Sec61 lateral gate, or is its role purely structural/scaffolding?

Q: Is the ER calcium homeostasis phenotype of CCDC47 deficiency a direct consequence of its Ca2+-binding capacity, or an indirect result of impaired biogenesis of calcium-handling membrane proteins?

Suggested Experiments

Experiment: Perform proteome-wide and targeted membrane-protein stability/surface-expression assays (e.g., dual-color ratiometric reporters) in CCDC47-knockout versus rescued cells across diverse client topologies.

Hypothesis: CCDC47 is required specifically for biogenesis of a defined set of multi-pass membrane proteins (GPCRs, channels, transporters) but not single-pass or tail-anchored proteins.

Type: cell-based membrane protein biogenesis assay

Experiment: Quantify ER calcium stores and IP3R/SOCE-mediated signaling in CCDC47-null cells rescued with wild-type CCDC47 versus a Ca2+-binding-deficient mutant, and measure abundance/localization of key ER calcium channels.

Hypothesis: The ER calcium defect in CCDC47-deficient cells is secondary to mislocalization/instability of calcium-handling multi-pass channels rather than to direct loss of CCDC47 Ca2+ buffering.

Type: calcium imaging with structure-function rescue

πŸ“š Additional Documentation

Notes

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Pn Notes

(CCDC47-pn-notes.md)

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